Literature DB >> 15742215

NR2A and NR2B receptor gene variations modify age at onset in Huntington disease.

Larissa Arning1, Peter H Kraus, Sandra Valentin, Carsten Saft, Jürgen Andrich, Jörg T Epplen.   

Abstract

N -Methyl-d-aspartate (NMDA) receptor-mediated excitotoxicity has been proposed to play a role in the pathogenesis of Huntington disease (HD), an autosomal dominantly inherited disorder associated with defined expansions in a stretch of perfect CAG repeats in the 5' part of the IT15 gene. The number of CAG repeat units is highly predictive for the age at onset (AO) in HD. However, AO is only modestly correlated with repeat length when the HD expansion range is in the high 30s or low 40s. Therefore, we investigated whether the genes for the different subunits composing the multimeric complexes of NMDA receptors (GRIN glutamate receptor, ionotropic, N-methyl-d-aspartate) represent candidates for modulating the AO of HD. In the studied cohort of 167 HD patients, the repeat range from 41 to 45 CAG units accounted for 30.8% of the variance in AO; 12.3% additional variance could be attributed to GRIN2B genotype variation and 4.5% to GRIN2A genotype variation. We conclude that these two genes, coding for NR2B and NR2A subtypes mainly expressed in the striatum, may influence the variability in AO of HD. Neuroprotective strategies for HD patients and persons at risk should be reconsidered in the light of these findings.

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Year:  2004        PMID: 15742215     DOI: 10.1007/s10048-004-0198-8

Source DB:  PubMed          Journal:  Neurogenetics        ISSN: 1364-6745            Impact factor:   2.660


  15 in total

Review 1.  Ligand-gated ion channel interactions with cytoskeletal and signaling proteins.

Authors:  M Sheng; D T Pak
Journal:  Annu Rev Physiol       Date:  2000       Impact factor: 19.318

2.  Loss of striatal serotonin synaptic receptor binding induced by kainic acid lesions: correlations with Huntington's Disease.

Authors:  R Schwarcz; J P Bennett; J T Coyle
Journal:  J Neurochem       Date:  1977-04       Impact factor: 5.372

3.  Polyglutamine-expanded huntingtin promotes sensitization of N-methyl-D-aspartate receptors via post-synaptic density 95.

Authors:  Y Sun; A Savanenin; P H Reddy; Y F Liu
Journal:  J Biol Chem       Date:  2001-04-23       Impact factor: 5.157

4.  Genotypes at the GluR6 kainate receptor locus are associated with variation in the age of onset of Huntington disease.

Authors:  D C Rubinsztein; J Leggo; M Chiano; A Dodge; G Norbury; E Rosser; D Craufurd
Journal:  Proc Natl Acad Sci U S A       Date:  1997-04-15       Impact factor: 11.205

5.  Age of onset in Huntington disease: sex specific influence of apolipoprotein E genotype and normal CAG repeat length.

Authors:  P Kehoe; M Krawczak; P S Harper; M J Owen; A L Jones
Journal:  J Med Genet       Date:  1999-02       Impact factor: 6.318

6.  Evidence for the GluR6 gene associated with younger onset age of Huntington's disease.

Authors:  M E MacDonald; J P Vonsattel; J Shrinidhi; N N Couropmitree; L A Cupples; E D Bird; J F Gusella; R H Myers
Journal:  Neurology       Date:  1999-10-12       Impact factor: 9.910

7.  A new polymerase chain reaction (PCR) assay for the trinucleotide repeat that is unstable and expanded on Huntington's disease chromosomes.

Authors:  J P Warner; L H Barron; D J Brock
Journal:  Mol Cell Probes       Date:  1993-06       Impact factor: 2.365

8.  New genomic region for Wegener's granulomatosis as revealed by an extended association screen with 202 apoptosis-related genes.

Authors:  Peter Jagiello; Martin Gencik; Larissa Arning; Stefan Wieczorek; Erdmute Kunstmann; Elena Csernok; Wolfgang L Gross; Joerg T Epplen
Journal:  Hum Genet       Date:  2004-02-14       Impact factor: 4.132

9.  Amino acid neurotransmitter abnormalities in Huntington's disease and the quinolinic acid animal model of Huntington's disease.

Authors:  D W Ellison; M F Beal; M F Mazurek; J R Malloy; E D Bird; J B Martin
Journal:  Brain       Date:  1987-12       Impact factor: 13.501

10.  Glutathione S-Transferase Omega 1 variation does not influence age at onset of Huntington's disease.

Authors:  Larissa Arning; Peter Jagiello; Stefan Wieczorek; Carsten Saft; Jürgen Andrich; Jörg T Epplen
Journal:  BMC Med Genet       Date:  2004-03-24       Impact factor: 2.103

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  37 in total

Review 1.  The Functional and Molecular Properties, Physiological Functions, and Pathophysiological Roles of GluN2A in the Central Nervous System.

Authors:  Yongjun Sun; Xiaokun Cheng; Linan Zhang; Jie Hu; You Chen; Liying Zhan; Zibin Gao
Journal:  Mol Neurobiol       Date:  2016-01-21       Impact factor: 5.590

2.  Replication of twelve association studies for Huntington's disease residual age of onset in large Venezuelan kindreds.

Authors:  J M Andresen; J Gayán; S S Cherny; D Brocklebank; G Alkorta-Aranburu; E A Addis; L R Cardon; D E Housman; N S Wexler
Journal:  J Med Genet       Date:  2006-10-03       Impact factor: 6.318

3.  Death of neuronal clusters contributes to variance of age at onset in Huntington's disease.

Authors:  Branka Cajavec; Hanspeter Herzel; Samuel Bernard
Journal:  Neurogenetics       Date:  2006-01-14       Impact factor: 2.660

4.  Genome-wide association study of severity in multiple sclerosis.

Authors: 
Journal:  Genes Immun       Date:  2011-06-09       Impact factor: 2.676

5.  Corticostriatal dysfunction and glutamate transporter 1 (GLT1) in Huntington's disease: interactions between neurons and astrocytes.

Authors:  Ana María Estrada-Sánchez; George V Rebec
Journal:  Basal Ganglia       Date:  2012-07-01

6.  SorCS2-mediated NR2A trafficking regulates motor deficits in Huntington's disease.

Authors:  Qian Ma; Jianmin Yang; Teresa A Milner; Jean-Paul G Vonsattel; Mary Ellen Palko; Lino Tessarollo; Barbara L Hempstead
Journal:  JCI Insight       Date:  2017-05-04

7.  Differential susceptibility to excitotoxic stress in YAC128 mouse models of Huntington disease between initiation and progression of disease.

Authors:  Rona K Graham; Mahmoud A Pouladi; Prasad Joshi; Ge Lu; Yu Deng; Nan-Ping Wu; Bryan E Figueroa; Martina Metzler; Véronique M André; Elizabeth J Slow; Lynn Raymond; Robert Friedlander; Michael S Levine; Blair R Leavitt; Michael R Hayden
Journal:  J Neurosci       Date:  2009-02-18       Impact factor: 6.167

8.  NR2A and NR2B receptor gene variations modify age at onset in Huntington disease in a sex-specific manner.

Authors:  Larissa Arning; Carsten Saft; Stefan Wieczorek; Jürgen Andrich; Peter H Kraus; Jörg T Epplen
Journal:  Hum Genet       Date:  2007-06-14       Impact factor: 4.132

9.  Subtype-selective antagonism of N-methyl-D-aspartate receptor ion channels by synthetic conantokin peptides.

Authors:  Zhenyu Sheng; Qiuyun Dai; Mary Prorok; Francis J Castellino
Journal:  Neuropharmacology       Date:  2007-05-10       Impact factor: 5.250

10.  Huntington's disease: the case for genetic modifiers.

Authors:  James F Gusella; Marcy E MacDonald
Journal:  Genome Med       Date:  2009-08-21       Impact factor: 11.117

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