| Literature DB >> 1550586 |
K Sukegawa1, S Tomatsu, K Tamai, M Ikeda, T Sasaki, M Masue, S Fukuda, Y Yamada, T Orii.
Abstract
Hunter disease, an X-linked recessive lysosomal storage disorder, is caused by a deficiency in iduronate sulfatase activity. Sequence analysis of mRNA of fibroblasts of an intermediate phenotype patient showed a single C1327 to T nucleotide transition. This mutation resulted in a substitution of termination codon for normal arginine at position 443 of the peptide sequence. Expression studies with this abnormal cDNA in fibroblasts from the patient revealed a loss of enzymatic activity and instability of the mutated protein. We posturate that this mutation is probably the cause of the intermediate form of Hunter disease.Entities:
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Year: 1992 PMID: 1550586 DOI: 10.1016/0006-291x(92)90555-y
Source DB: PubMed Journal: Biochem Biophys Res Commun ISSN: 0006-291X Impact factor: 3.575