Literature DB >> 1550184

Abnormal rod dark adaptation in autosomal dominant retinitis pigmentosa with proline-23-histidine rhodopsin mutation.

C M Kemp1, S G Jacobson, A J Roman, C H Sung, J Nathans.   

Abstract

We studied rod and cone function in 13 patients from four families with autosomal dominant retinitis pigmentosa and the proline-23-histidine rhodopsin mutation. In patients with early stages of this disease, rod sensitivity was mildly abnormal throughout the retina and cone sensitivity was normal. In more severely affected patients, sensitivity loss varied with retinal region, some regions showing mild rod loss only and other regions having pronounced rod and cone dysfunction. Rhodopsin levels were decreased below normal by amounts that indicated the rod sensitivity loss was determined by the reduced ability to absorb light. The most characteristic abnormality of this genotype was a slowed rod branch of dark adaptation, which was present regardless of the extent or severity of disease. The time required for recovery of rod sensitivity was more than twice the normal time. These findings with dark-adapted perimetry, fundus reflectometry, and dark adaptometry showed intrafamilial and interfamilial consistency.

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Year:  1992        PMID: 1550184     DOI: 10.1016/s0002-9394(14)71529-6

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  25 in total

1.  Nine generations of a family with autosomal dominant retinitis pigmentosa and evidence of variable expressivity from census records.

Authors:  M Jay; A C Bird; A N Moore; B Jay
Journal:  J Med Genet       Date:  1992-12       Impact factor: 6.318

Review 2.  Light and inherited retinal degeneration.

Authors:  D M Paskowitz; M M LaVail; J L Duncan
Journal:  Br J Ophthalmol       Date:  2006-05-17       Impact factor: 4.638

Review 3.  Retinitis pigmentosa: unfolding its mystery.

Authors:  E L Berson
Journal:  Proc Natl Acad Sci U S A       Date:  1996-05-14       Impact factor: 11.205

4.  Constitutive "light" adaptation in rods from G90D rhodopsin: a mechanism for human congenital nightblindness without rod cell loss.

Authors:  P A Sieving; M L Fowler; R A Bush; S Machida; P D Calvert; D G Green; C L Makino; C L McHenry
Journal:  J Neurosci       Date:  2001-08-01       Impact factor: 6.167

5.  Dark adaptation in retinal abnormalities.

Authors:  F W Fitzke
Journal:  Br J Ophthalmol       Date:  1994-06       Impact factor: 4.638

6.  Steroids do not prevent photoreceptor degeneration in the light-exposed T4R rhodopsin mutant dog retina irrespective of AP-1 inhibition.

Authors:  Danian Gu; William A Beltran; Sue Pearce-Kelling; Zexiao Li; Gregory M Acland; Gustavo D Aguirre
Journal:  Invest Ophthalmol Vis Sci       Date:  2009-02-21       Impact factor: 4.799

Review 7.  Finding and interpreting genetic variations that are important to ophthalmologists.

Authors:  Edwin M Stone
Journal:  Trans Am Ophthalmol Soc       Date:  2003

8.  Xenopus laevis P23H rhodopsin transgene causes rod photoreceptor degeneration that is more severe in the ventral retina and is modulated by light.

Authors:  Rui Zhang; Ericka Oglesby; Nicholas Marsh-Armstrong
Journal:  Exp Eye Res       Date:  2008-01-12       Impact factor: 3.467

Review 9.  Gene augmentation for adRP mutations in RHO.

Authors:  Alfred S Lewin; Brian Rossmiller; Haoyu Mao
Journal:  Cold Spring Harb Perspect Med       Date:  2014-07-18       Impact factor: 6.915

10.  Disease sequence from mutant rhodopsin allele to rod and cone photoreceptor degeneration in man.

Authors:  A V Cideciyan; D C Hood; Y Huang; E Banin; Z Y Li; E M Stone; A H Milam; S G Jacobson
Journal:  Proc Natl Acad Sci U S A       Date:  1998-06-09       Impact factor: 11.205

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