Literature DB >> 15165675

Laryngeal dystonia in a case of severe motor and intellectual disabilities due to Japanese encephalitis sequelae.

Kimiko Hamano1, Satoko Kumada, Masaharu Hayashi, Rie Naito, Tetsuro Hayashida, Akira Uchiyama, Kiyoko Kurata.   

Abstract

Laryngeal dystonia is characterized by stridor due to vocal cord dystonia and is observed in extrapyramidal disorders. Recently, botulinum toxin injection has been used as a primary therapy. Generally, severe motor and intellectual disabilities (SMID) are frequently complicated by various types of respiratory disorders. We report a SMID case with Japanese encephalitis sequelae showing repeated vocal cord abductor disturbance due to laryngeal dystonia, in addition to generalized dystonia, in whom MRI revealed basal ganglia lesions. Tracheostomy was effective for the case, and we believe that botulinum toxin injection may be inappropriate in SMID, both ethically and technically. Also, laryngeal dystonia should be considered as a cause of respiratory disorders in SMID.

Entities:  

Mesh:

Year:  2004        PMID: 15165675     DOI: 10.1016/S0387-7604(03)00194-3

Source DB:  PubMed          Journal:  Brain Dev        ISSN: 0387-7604            Impact factor:   1.961


  2 in total

1.  Childhood Laryngeal Dystonia Following Bilateral Globus Pallidus Abnormality: A Case Study and Review of Literature.

Authors:  Mohammad Javad Saeedi Borujeni; Ebrahim Esfandiary; Mostafa Almasi-Dooghaee
Journal:  Iran J Otorhinolaryngol       Date:  2017-01

Review 2.  Clinical spectrum and management of dystonia in patients with Japanese encephalitis: A systematic review.

Authors:  Roshan Aryal; Suraj Shrestha; Sushan Homagain; Sunit Chhetri; Kshitiz Shrestha; Sanjeev Kharel; Ragesh Karn; Reema Rajbhandari; Bikram Prasad Gajurel; Rajeev Ojha
Journal:  Brain Behav       Date:  2022-01-13       Impact factor: 2.708

  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.