Literature DB >> 15151509

Bronchiectasis in adult patients: an expression of heterozygosity for CFTR gene mutations?

T Casals1, J De-Gracia, M Gallego, J Dorca, B Rodríguez-Sanchón, M D Ramos, J Giménez, A Cisteró-Bahima, C Olveira, X Estivill.   

Abstract

While all patients with cystic fibrosis (CF) have mutations in both CFTR alleles, often only one CFTR change is detected in patients with other lung disorders. The aim of this study was to investigate whether heterozygosity for CFTR mutations could be a determinant risk factor in the development of bronchiectasis in adult patients. We have performed the CFTR gene analysis in a cohort of 55 bronchiectasis adult patients with unknown etiology. The 5T variant (TG)m and the M470V polymorphisms were also analyzed. A general population in which the same molecular analysis was previously performed was used as the control group. The mutational spectrum of patients was also compared with that found in our CF population. CFTR mutations/variants were found in 20 patients (36%), 14 with only one mutant gene (25%). All six patients colonized by Staphylococcus aureus presented with at least one CFTR change (p = 0.001). No statistical significance was observed between patients with and without mutations for other clinical features. The 5T variant was found in four patients. Additionally, 90% of patients with mutations had the more functional M470 allele (p < 0.001). These results suggest the involvement of the CFTR gene in bronchiectasis of unknown etiology in adult patients.

Entities:  

Mesh:

Substances:

Year:  2004        PMID: 15151509     DOI: 10.1111/j.0009-9163.2004.00265.x

Source DB:  PubMed          Journal:  Clin Genet        ISSN: 0009-9163            Impact factor:   4.438


  21 in total

1.  Increased Risk of Interstitial Lung Disease in Children with a Single R288K Variant of ABCA3.

Authors:  Thomas Wittmann; Sabrina Frixel; Stefanie Höppner; Ulrike Schindlbeck; Andrea Schams; Matthias Kappler; Jan Hegermann; Christoph Wrede; Gerhard Liebisch; Anne Vierzig; Angela Zacharasiewicz; Matthias Volkmar Kopp; Christian F Poets; Winfried Baden; Dominik Hartl; Anton H van Kaam; Peter Lohse; Charalampos Aslanidis; Ralf Zarbock; Matthias Griese
Journal:  Mol Med       Date:  2016-02-26       Impact factor: 6.354

2.  Genotype-phenotype correlation for pulmonary function in cystic fibrosis.

Authors:  J de Gracia; F Mata; A Alvarez; T Casals; S Gatner; M Vendrell; D de la Rosa; L Guarner; E Hermosilla
Journal:  Thorax       Date:  2005-07       Impact factor: 9.139

Review 3.  Precision Genomic Medicine in Cystic Fibrosis.

Authors:  Eugene H Chang; Joseph Zabner
Journal:  Clin Transl Sci       Date:  2015-06-15       Impact factor: 4.689

4.  p.Ser1235Arg should no longer be considered as a cystic fibrosis mutation: results from a large collaborative study.

Authors:  Céline René; Damien Paulet; Emmanuelle Girodon; Catherine Costa; Guy Lalau; Julie Leclerc; Faïza Cabet-Bey; Thierry Bienvenu; Martine Blayau; Albert Iron; Hervé Mittre; Delphine Feldmann; Caroline Guittard; Mireille Claustres; Marie des Georges
Journal:  Eur J Hum Genet       Date:  2010-08-18       Impact factor: 4.246

Review 5.  Pathophysiology and Genetics of Bronchiectasis Unrelated to Cystic Fibrosis.

Authors:  Aleksandra Nikolic
Journal:  Lung       Date:  2018-05-12       Impact factor: 2.584

Review 6.  Consensus on the use and interpretation of cystic fibrosis mutation analysis in clinical practice.

Authors:  C Castellani; H Cuppens; M Macek; J J Cassiman; E Kerem; P Durie; E Tullis; B M Assael; C Bombieri; A Brown; T Casals; M Claustres; G R Cutting; E Dequeker; J Dodge; I Doull; P Farrell; C Ferec; E Girodon; M Johannesson; B Kerem; M Knowles; A Munck; P F Pignatti; D Radojkovic; P Rizzotti; M Schwarz; M Stuhrmann; M Tzetis; J Zielenski; J S Elborn
Journal:  J Cyst Fibros       Date:  2008-05       Impact factor: 5.482

7.  Comparative analysis of common CFTR polymorphisms poly-T, TG-repeats and M470V in a healthy Chinese population.

Authors:  Qin Huang; Wei Ding; Mu-Xin Wei
Journal:  World J Gastroenterol       Date:  2008-03-28       Impact factor: 5.742

8.  Assessing the Disease-Liability of Mutations in CFTR.

Authors:  Claude Ferec; Garry R Cutting
Journal:  Cold Spring Harb Perspect Med       Date:  2012-12-01       Impact factor: 6.915

9.  Analysis of CFTR Gene Variants in Idiopathic Bronchiectasis in Serbian Children.

Authors:  Katarina Milosevic; Aleksandra Nikolic; Aleksandra Divac Rankov; Mila Ljujic; Branimir Nestorovic; Dragica Radojkovic
Journal:  Pediatr Allergy Immunol Pulmonol       Date:  2013-06       Impact factor: 1.349

10.  Next-generation sequencing for identifying genetic mutations in adults with bronchiectasis.

Authors:  Wei-Jie Guan; Jia-Cheng Li; Fang Liu; Jian Zhou; Ya-Ping Liu; Chao Ling; Yong-Hua Gao; Hui-Min Li; Jing-Jing Yuan; Yan Huang; Chun-Lan Chen; Rong-Chang Chen; Xue Zhang; Nan-Shan Zhong
Journal:  J Thorac Dis       Date:  2018-05       Impact factor: 2.895

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.