Literature DB >> 15100373

Results of a nationwide screening for Anderson-Fabry disease among dialysis patients.

Peter Kotanko1, Reinhard Kramar, Danijela Devrnja, Eduard Paschke, Till Voigtländer, Martin Auinger, Severo Pagliardini, Marco Spada, Klaus Demmelbauer, Matthias Lorenz, Anna-Christine Hauser, Hans-Jörg Kofler, Karl Lhotta, Ulrich Neyer, Wolfgang Pronai, Manfred Wallner, Clemens Wieser, Martin Wiesholzer, Herbert Zodl, Manuela Födinger, Gere Sunder-Plassmann.   

Abstract

Anderson-Fabry disease is possibly underdiagnosed in patients with end-stage renal disease. Nationwide screening was therefore undertaken for Anderson-Fabry disease among dialysis patients in Austria. Screening for alpha-galactosidase A (AGAL) deficiency was performed by a blood spot test. In patients with a positive screening test, AGAL activity in leukocytes was determined. Individuals with decreased leukocyte AGAL activity were subjected to mutation testing in the GLA gene. Fifty (90.9%) of 55 Austrian hemodialysis centers participated in this study; 2480 dialysis patients (80.1% of the Austrian dialysis population) were screened. In 85 patients, the screening test was positive (85 of 2480, 3.42%; women, 3.32%; men, 3.50%). Among these 85 patients, 4 men (in 3 of whom Anderson-Fabry disease was already known before screening) had a severely decreased and 11 subjects had a borderline low AGAL activity. Genetic testing revealed mutations associated with Fabry disease in all four men with severely decreased AGAL activity resulting in a prevalence of 0.161% for the entire study population. A nationwide screening of dialysis patients permitted detection of a hitherto unknown man with Anderson-Fabry disease. The overall prevalence among dialysis patients was at least ten times higher as compared with recent registry data. Screening programs among patients with end-stage renal disease, especially men, should be put in place to identify families with Anderson-Fabry disease who probably may benefit from specific clinical care, and perhaps from enzyme replacement therapy. In dialysis patients, however, there is no evidence to support enzyme replacement therapy at present.

Entities:  

Mesh:

Substances:

Year:  2004        PMID: 15100373     DOI: 10.1097/01.asn.0000124671.61963.1e

Source DB:  PubMed          Journal:  J Am Soc Nephrol        ISSN: 1046-6673            Impact factor:   10.121


  52 in total

1.  High prevalence of subclinical hypothyroidism in patients with Anderson-Fabry disease.

Authors:  A C Hauser; A Gessl; M Lorenz; T Voigtländer; M Födinger; G Sunder-Plassmann
Journal:  J Inherit Metab Dis       Date:  2005       Impact factor: 4.982

2.  Prevalence of Fabry disease in male patients with unexplained left ventricular hypertrophy in primary cardiology practice: prospective Fabry cardiomyopathy screening study (FACSS).

Authors:  Tomas Palecek; Jitka Honzikova; Helena Poupetova; Hana Vlaskova; Petr Kuchynka; Lubor Golan; Sudheera Magage; Ales Linhart
Journal:  J Inherit Metab Dis       Date:  2013-10-31       Impact factor: 4.982

3.  Significance of screening for Fabry disease among male dialysis patients.

Authors:  Mayuri Ichinose; Masaaki Nakayama; Toya Ohashi; Yasunori Utsunomiya; Masahisa Kobayashi; Yoshikatsu Eto
Journal:  Clin Exp Nephrol       Date:  2005-09       Impact factor: 2.801

4.  Frequency of unrecognized Fabry disease among young European-American and African-American men with first ischemic stroke.

Authors:  Marcella A Wozniak; Steven J Kittner; Stanley Tuhrim; John W Cole; Barney Stern; Mark Dobbins; Marie E Grace; Irina Nazarenko; Robert Dobrovolny; Eric McDade; Robert J Desnick
Journal:  Stroke       Date:  2009-12-10       Impact factor: 7.914

Review 5.  Enzyme replacement therapy of Fabry disease.

Authors:  Joe T R Clarke; R Mark Iwanochko
Journal:  Mol Neurobiol       Date:  2005-08       Impact factor: 5.590

6.  Early diagnosis of fabry disease in a patient with toe tip pain.

Authors:  Ki Bum Park; Kyung Ream Han; Jae Woo Lee; Seung Ho Kim; Do Wan Kim; Chan Kim; Jung Min Ko
Journal:  Korean J Pain       Date:  2010-08-26

7.  The birth prevalence of lysosomal storage disorders in the Czech Republic: comparison with data in different populations.

Authors:  Helena Poupetová; Jana Ledvinová; Linda Berná; Lenka Dvoráková; Viktor Kozich; Milan Elleder
Journal:  J Inherit Metab Dis       Date:  2010-05-20       Impact factor: 4.982

Review 8.  Fabry disease: raising awareness of the disease among physicians.

Authors:  Francesca Carubbi; Lisa Bonilauri
Journal:  Intern Emerg Med       Date:  2012-10       Impact factor: 3.397

Review 9.  Fabry disease-often seen, rarely diagnosed.

Authors:  Björn Hoffmann; Ertan Mayatepek
Journal:  Dtsch Arztebl Int       Date:  2009-06-26       Impact factor: 5.594

10.  Newborn screening for Fabry disease in Taiwan reveals a high incidence of the later-onset GLA mutation c.936+919G>A (IVS4+919G>A).

Authors:  Wuh-Liang Hwu; Yin-Hsiu Chien; Ni-Chung Lee; Shu-Chuan Chiang; Robert Dobrovolny; Ai-Chu Huang; Hui-Ying Yeh; May-Chin Chao; Shio-Jean Lin; Teruo Kitagawa; Robert J Desnick; Li-Wen Hsu
Journal:  Hum Mutat       Date:  2009-10       Impact factor: 4.878

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.