Literature DB >> 15000811

Multiplex ligation-dependent probe amplification (MLPA) detects large deletions in the MECP2 gene of Swedish Rett syndrome patients.

Anna Erlandson1, Lena Samuelsson, Bengt Hagberg, Mårten Kyllerman, Mihailo Vujic, Jan Wahlström.   

Abstract

Mutations in the methyl-CpG-binding protein-2 (MECP2) gene on Xq28 have been found to be a cause of Rett syndrome (RS). In a previous mutation screening, we found MECP2 mutations in 81% of Swedish classical Rett women. In this study, we have analyzed 22 patients for MECP2 deletions using multiplex-ligation-dependent probe amplification (MLPA). Clinically, 11 of the patients who were classical Rett women, 3 were forme fruste, 1 was congenital RS, and 7 were Rett variants. As inclusion criteria, we used DNA from patients in whom previous sequencing results showed no mutations in coding portions of the MECP2 gene. MLPA is a method based on multiplex PCR. In one PCR, as many as 40 probes are amplified with the same primers. The specificity of the amplification products is determined by the site-specific hybridization of each probe construct, prior to amplification. Each PCR product has a unique length, which makes it possible to identify it by size separation. In 3 of 11 (27%) classical Rett women, we detected large deletions in MECP2 using MLPA. All these patients had deletions covering two exons; in 2 cases the deletion involved exons 3 and 4 and, in one case, exons 1 and 2 were missing. In the forme fruste, congenital and Rett-variant patients, we found no large deletions. We have found that MLPA is useful when it comes to finding large deletions compromising whole exons in MECP2. Used as a complementary method to DNA sequencing, it revealed new MECP2 mutations in classical RS patients.

Entities:  

Mesh:

Substances:

Year:  2003        PMID: 15000811     DOI: 10.1089/109065703322783707

Source DB:  PubMed          Journal:  Genet Test        ISSN: 1090-6576


  25 in total

1.  The phenotype associated with a large deletion on MECP2.

Authors:  Ami Bebbington; Jenny Downs; Alan Percy; Mercé Pineda; Bruria Ben Zeev; Nadia Bahi-Buisson; Helen Leonard
Journal:  Eur J Hum Genet       Date:  2012-04-04       Impact factor: 4.246

Review 2.  Rett syndrome: clinical review and genetic update.

Authors:  L S Weaving; C J Ellaway; J Gécz; J Christodoulou
Journal:  J Med Genet       Date:  2005-01       Impact factor: 6.318

Review 3.  Rett syndrome and the impact of MeCP2 associated transcriptional mechanisms on neurotransmission.

Authors:  Lisa M Monteggia; Ege T Kavalali
Journal:  Biol Psychiatry       Date:  2008-12-05       Impact factor: 13.382

4.  Inherited human IRAK-1 deficiency selectively impairs TLR signaling in fibroblasts.

Authors:  Erika Della Mina; Alessandro Borghesi; Hao Zhou; Salim Bougarn; Sabri Boughorbel; Laura Israel; Ilaria Meloni; Maya Chrabieh; Yun Ling; Yuval Itan; Alessandra Renieri; Iolanda Mazzucchelli; Sabrina Basso; Piero Pavone; Raffaele Falsaperla; Roberto Ciccone; Rosa Maria Cerbo; Mauro Stronati; Capucine Picard; Orsetta Zuffardi; Laurent Abel; Damien Chaussabel; Nico Marr; Xiaoxia Li; Jean-Laurent Casanova; Anne Puel
Journal:  Proc Natl Acad Sci U S A       Date:  2017-01-09       Impact factor: 11.205

5.  Gross rearrangements of the MECP2 gene are found in both classical and atypical Rett syndrome patients.

Authors:  H L Archer; S D Whatley; J C Evans; D Ravine; P Huppke; A Kerr; D Bunyan; B Kerr; E Sweeney; S J Davies; W Reardon; J Horn; K D MacDermot; R A Smith; A Magee; A Donaldson; Y Crow; G Hermon; Z Miedzybrodzka; D N Cooper; L Lazarou; R Butler; J Sampson; D T Pilz; F Laccone; A J Clarke
Journal:  J Med Genet       Date:  2005-09-23       Impact factor: 6.318

6.  Comprehensive diagnosis of Rett's syndrome relying on genetic, epigenetic and expression evidence of deficiency of the methyl-CpG-binding protein 2 gene: study of a cohort of Israeli patients.

Authors:  Y Petel-Galil; B Benteer; Y P Galil; B B Zeev; I Greenbaum; M Vecsler; B Goldman; H Lohi; B A Minassian; E Gak
Journal:  J Med Genet       Date:  2006-12       Impact factor: 6.318

Review 7.  Atypical Rett syndrome with selective FOXG1 deletion detected by comparative genomic hybridization: case report and review of literature.

Authors:  Francois Dominique Jacob; Vijay Ramaswamy; John Andersen; Francois V Bolduc
Journal:  Eur J Hum Genet       Date:  2009-07-22       Impact factor: 4.246

Review 8.  Copy number variation in human health, disease, and evolution.

Authors:  Feng Zhang; Wenli Gu; Matthew E Hurles; James R Lupski
Journal:  Annu Rev Genomics Hum Genet       Date:  2009       Impact factor: 8.929

9.  Development of multiplex assay for rapid characterization of Mycobacterium tuberculosis.

Authors:  I L Bergval; R N C P Vijzelaar; E R Dalla Costa; A R J Schuitema; L Oskam; A L Kritski; P R Klatser; R M Anthony
Journal:  J Clin Microbiol       Date:  2007-12-12       Impact factor: 5.948

10.  Comparison of different techniques for the detection of genetic risk-identifying chromosomal gains and losses in neuroblastoma.

Authors:  Eva Villamón; Marta Piqueras; Carlos Mackintosh; Javier Alonso; Enrique de Alava; Samuel Navarro; Rosa Noguera
Journal:  Virchows Arch       Date:  2008-06-24       Impact factor: 4.064

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.