Literature DB >> 14961910

Granulomas in common variable immunodeficiency: a diagnostic dilemma.

Karyn R Lun1, Dominic J Wood, James B Muir, Rowland Noakes.   

Abstract

A 60-year-old man with common variable immunodeficiency presented with a 7-year history of violaceous plaques and papules on the thighs, arms and trunk. In the preceding 2 years he had developed new lesions on both hands. He had been previously diagnosed with sarcoidosis on the basis of skin and visceral histology, but subsequent opinion was that these were sarcoid-like granulomas rather than being representative of true sarcoidosis. Biopsy of the hand lesions showed necrotizing granulomas, and a single acid-fast bacillus (AFB) was identified on Wade-Fite stain. Subsequent repeat tissue biopsies for histology, culture and polymerase chain reaction testing failed to confirm the presence of mycobacterial organisms and it was felt that the organism was a contaminant introduced during tissue processing. The hand lesions responded well to intralesional injections of triamcinolone acetonide 10 mg/mL and oral tetracycline 500 mg b.d. was later introduced with a good clinical response. The diagnostic dilemma of finding granulomatous inflammation in a patient with common variable immunodeficiency, and the significance of a single AFB on histology are discussed. The treatment of sarcoid-like granulomas with tetracycline therapy is also commented on.

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Year:  2004        PMID: 14961910     DOI: 10.1111/j.1440-0960.2004.00031.x

Source DB:  PubMed          Journal:  Australas J Dermatol        ISSN: 0004-8380            Impact factor:   2.875


  5 in total

1.  CTLA-4 gene exon-1 +49 A/G polymorphism: lack of association with autoimmune disease in patients with common variable immune deficiency.

Authors:  Adina Kay Knight; Davide Serrano; Yaron Tomer; Charlotte Cunningham-Rundles
Journal:  J Clin Immunol       Date:  2006-12-28       Impact factor: 8.317

Review 2.  Granulomatous disease in CVID: retrospective analysis of clinical characteristics and treatment efficacy in a cohort of 59 patients.

Authors:  Jean-Nicolas Boursiquot; Laurence Gérard; Marion Malphettes; Claire Fieschi; Lionel Galicier; David Boutboul; Raphael Borie; Jean-François Viallard; Pauline Soulas-Sprauel; Alice Berezne; Arnaud Jaccard; Eric Hachulla; Julien Haroche; Nicolas Schleinitz; Laurent Têtu; Eric Oksenhendler
Journal:  J Clin Immunol       Date:  2012-09-18       Impact factor: 8.317

Review 3.  Granulomatous disease in common variable immunodeficiency.

Authors:  Yoshikazu Morimoto; John M Routes
Journal:  Curr Allergy Asthma Rep       Date:  2005-09       Impact factor: 4.919

4.  What Works When Treating Granulomatous Disease in Genetically Undefined CVID? A Systematic Review.

Authors:  Astrid C van Stigt; Willem A Dik; Lieke S J Kamphuis; Bas M Smits; Joris M van Montfrans; P Martin van Hagen; Virgil A S H Dalm; Hanna IJspeert
Journal:  Front Immunol       Date:  2020-12-17       Impact factor: 7.561

5.  Cutaneous sarcoid-like granulomas in a child known with nijmegen breakage syndrome.

Authors:  Rachisan Andreea Liana; Gheban Dan; Miu Nicolae
Journal:  Iran J Pediatr       Date:  2013-02       Impact factor: 0.364

  5 in total

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