Literature DB >> 1431990

Use of single strand conformation polymorphism analysis to detect point mutations in human mitochondrial DNA.

A Suomalainen1, E Ciafaloni, Y Koga, L Peltonen, S DiMauro, E A Schon.   

Abstract

Myoclonus epilepsy with ragged-red fibers (MERRF) has been shown to be associated with a specific point mutation at the nucleotide 8344 in the tRNA(Lys) gene of mitochondrial DNA (mtDNA). We screened 6 patients with clinically diagnosed MERRF and 1 patient with ocular myopathy for point mutations in the tRNA(Lys) gene, using single strand conformation polymorphism (SSCP) analysis, which can detect even a 1-basepair difference between 2 DNA sequences. Using SSCP and consequent DNA sequencing, we identified the known MERRF mutation in 4 out of 6 MERRF patients, as well as in 1 patient with a new clinical phenotype associated with this mutation: progressive external ophthalmoplegia, muscle weakness and a lipoma, but no myoclonus or epilepsy. Two of the patients with clinical MERRF had neither the MERRF-mutation nor any other mutations in the tRNA(Lys) gene. Using SSCP analysis, we also detected a new polymorphism in 1 patient. Thus, SSCP analysis can be applied to search effectively and rapidly for point mutations or polymorphisms in mitochondrial DNA.

Entities:  

Mesh:

Substances:

Year:  1992        PMID: 1431990     DOI: 10.1016/0022-510x(92)90074-u

Source DB:  PubMed          Journal:  J Neurol Sci        ISSN: 0022-510X            Impact factor:   3.181


  5 in total

1.  Mutation analysis of the entire mitochondrial genome using denaturing high performance liquid chromatography.

Authors:  B J van Den Bosch; R F de Coo; H R Scholte; J G Nijland; R van Den Bogaard; M de Visser; C E de Die-Smulders; H J Smeets
Journal:  Nucleic Acids Res       Date:  2000-10-15       Impact factor: 16.971

2.  Maternally inherited cardiomyopathy and hearing loss associated with a novel mutation in the mitochondrial tRNA(Lys) gene (G8363A).

Authors:  F M Santorelli; S C Mak; M El-Schahawi; C Casali; S Shanske; T Z Baram; R E Madrid; S DiMauro
Journal:  Am J Hum Genet       Date:  1996-05       Impact factor: 11.025

3.  A disease-associated G5703A mutation in human mitochondrial DNA causes a conformational change and a marked decrease in steady-state levels of mitochondrial tRNA(Asn).

Authors:  H Hao; C T Moraes
Journal:  Mol Cell Biol       Date:  1997-12       Impact factor: 4.272

Review 4.  Investigation of muscle disease.

Authors:  F L Mastaglia; N G Laing
Journal:  J Neurol Neurosurg Psychiatry       Date:  1996-03       Impact factor: 10.154

Review 5.  The in-depth evaluation of suspected mitochondrial disease.

Authors:  Richard H Haas; Sumit Parikh; Marni J Falk; Russell P Saneto; Nicole I Wolf; Niklas Darin; Lee-Jun Wong; Bruce H Cohen; Robert K Naviaux
Journal:  Mol Genet Metab       Date:  2008-02-01       Impact factor: 4.797

  5 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.