Literature DB >> 1385966

Complete rescue of photoreceptor dysplasia and degeneration in transgenic retinal degeneration slow (rds) mice.

G H Travis1, K R Groshan, M Lloyd, D Bok.   

Abstract

retinal degeneration slow (rds) is a semidominant mutation of mice with the phenotype of abnormal development of rod and cone photoreceptors, followed by their slow degeneration. The rds gene has been putatively cloned and its novel protein product initially characterized biochemically. In the present study we undertook to correct in vivo the retinal phenotype of mice with the rds mutation. We assembled a transgene containing a regulatory segment of the opsin gene positioned upstream of the wild-type rds coding region. Mice from three transgenic lines, homozygous for the rds mutation, were analyzed for expression of the transgene and for their retinal phenotypes. In two high expressing lines, we observed complete reversion to wild-type retinal morphology. In a third, low expressing line, we observed a retinal phenotype intermediate between wild type and rds/rds, suggesting partial rescue of the mutation. These results constitute formal proof that we have cloned the rds gene.

Entities:  

Mesh:

Substances:

Year:  1992        PMID: 1385966     DOI: 10.1016/0896-6273(92)90226-4

Source DB:  PubMed          Journal:  Neuron        ISSN: 0896-6273            Impact factor:   17.173


  35 in total

Review 1.  Management of inherited outer retinal dystrophies: present and future.

Authors:  N H Chong; A C Bird
Journal:  Br J Ophthalmol       Date:  1999-01       Impact factor: 4.638

Review 2.  Photoreceptor renewal: a role for peripherin/rds.

Authors:  Kathleen Boesze-Battaglia; Andrew F X Goldberg
Journal:  Int Rev Cytol       Date:  2002

3.  Expression of Bcl-2 protects against photoreceptor degeneration in retinal degeneration slow (rds) mice.

Authors:  I Nir; W Kedzierski; J Chen; G H Travis
Journal:  J Neurosci       Date:  2000-03-15       Impact factor: 6.167

4.  Genetic supplementation of RDS alleviates a loss-of-function phenotype in C214S model of retinitis pigmentosa.

Authors:  May Nour; Steven J Fliesler; Muna I Naash
Journal:  Adv Exp Med Biol       Date:  2008       Impact factor: 2.622

5.  Overexpression of rhodopsin alters the structure and photoresponse of rod photoreceptors.

Authors:  Xiao-Hong Wen; Lixin Shen; Richard S Brush; Norman Michaud; Muayyad R Al-Ubaidi; Vsevolod V Gurevich; Heidi E Hamm; Janis Lem; Emmanuele Dibenedetto; Robert E Anderson; Clint L Makino
Journal:  Biophys J       Date:  2009-02       Impact factor: 4.033

6.  In situ visualization of protein interactions in sensory neurons: glutamic acid-rich proteins (GARPs) play differential roles for photoreceptor outer segment scaffolding.

Authors:  Linda M Ritter; Nidhi Khattree; Beatrice Tam; Orson L Moritz; Frank Schmitz; Andrew F X Goldberg
Journal:  J Neurosci       Date:  2011-08-03       Impact factor: 6.167

Review 7.  Cell loss in retinal dystrophies by apoptosis--death by informed consent!

Authors:  C Y Gregory; A C Bird
Journal:  Br J Ophthalmol       Date:  1995-02       Impact factor: 4.638

8.  Stable and efficient gene transfer into the retina using an HIV-based lentiviral vector.

Authors:  H Miyoshi; M Takahashi; F H Gage; I M Verma
Journal:  Proc Natl Acad Sci U S A       Date:  1997-09-16       Impact factor: 11.205

9.  An inducible amphipathic helix within the intrinsically disordered C terminus can participate in membrane curvature generation by peripherin-2/rds.

Authors:  Michelle L Milstein; Victoria A Kimler; Chiranjib Ghatak; Alexey S Ladokhin; Andrew F X Goldberg
Journal:  J Biol Chem       Date:  2017-03-21       Impact factor: 5.157

10.  A monogenic dominant mutation in Rom1 generated by N-ethyl-N-nitrosourea mutagenesis causes retinal degeneration in mice.

Authors:  Hajime Sato; Tomohiro Suzuki; Kyoko Ikeda; Hiroshi Masuya; Hideki Sezutsu; Hideki Kaneda; Kimio Kobayashi; Ikuo Miura; Yasuyuki Kurihara; Shunji Yokokura; Kohji Nishida; Makoto Tamai; Yoichi Gondo; Tetsuo Noda; Shigeharu Wakana
Journal:  Mol Vis       Date:  2010-03-10       Impact factor: 2.367

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.