Literature DB >> 12825077

Novel POLG mutations in progressive external ophthalmoplegia mimicking mitochondrial neurogastrointestinal encephalomyopathy.

Gert Van Goethem1, Marianne Schwartz, Ann Löfgren, Bart Dermaut, Christine Van Broeckhoven, John Vissing.   

Abstract

Autosomal recessive progressive external ophthalmoplegia (PEO) is one clinical disorder associated with multiple mitochondrial DNA deletions and can be caused by missense mutations in POLG, the gene encoding the mitochondrial DNA polymerase gamma. Mitochondrial neurogastrointestinal encephalomyopathy (MNGIE) is another autosomal recessive disorder associated with PEO and multiple deletions of mitochondrial DNA in skeletal muscle. In several patients this disorder is caused by loss of function mutations in the gene encoding thymidine phosphorylase (TP). We report a recessive family with features of MNGIE but no leukoencephalopathy in which two patients carry three missense mutations in POLG, of which two are novel mutations (N846S and P587L). The third mutation was previously reported as a recessive POLG mutation (T251I). This finding indicates the need for POLG sequencing in patients with features of MNGIE without TP mutations.

Entities:  

Mesh:

Substances:

Year:  2003        PMID: 12825077     DOI: 10.1038/sj.ejhg.5201002

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  35 in total

1.  Clinical and genetic spectrum of mitochondrial neurogastrointestinal encephalomyopathy.

Authors:  Caterina Garone; Saba Tadesse; Michio Hirano
Journal:  Brain       Date:  2011-09-20       Impact factor: 13.501

2.  Twinkle and POLG defects enhance age-dependent accumulation of mutations in the control region of mtDNA.

Authors:  Sjoerd Wanrooij; Petri Luoma; Gert van Goethem; Christine van Broeckhoven; Anu Suomalainen; Johannes N Spelbrink
Journal:  Nucleic Acids Res       Date:  2004-06-04       Impact factor: 16.971

3.  Synergistic Effects of the in cis T251I and P587L Mitochondrial DNA Polymerase γ Disease Mutations.

Authors:  Karen L DeBalsi; Matthew J Longley; Kirsten E Hoff; William C Copeland
Journal:  J Biol Chem       Date:  2017-02-02       Impact factor: 5.157

Review 4.  Mitochondrial disorders of DNA polymerase γ dysfunction: from anatomic to molecular pathology diagnosis.

Authors:  Linsheng Zhang; Sherine S L Chan; Daynna J Wolff
Journal:  Arch Pathol Lab Med       Date:  2011-07       Impact factor: 5.534

5.  Mitochondrial neurogastrointestinal encephalomyopathy (MNGIE)-like phenotype in a patient with a novel heterozygous POLG mutation.

Authors:  Pankaj Prasun; Dwight D Koeberl
Journal:  J Neurol       Date:  2014-07-15       Impact factor: 4.849

Review 6.  Mitochondrial disease in pregnancy: a systematic review.

Authors:  R E Say; R G Whittaker; H E Turnbull; R McFarland; R W Taylor; D M Turnbull
Journal:  Obstet Med       Date:  2011-06-23

Review 7.  Progressive external ophthalmoplegia characterized by multiple deletions of mitochondrial DNA: unraveling the pathogenesis of human mitochondrial DNA instability and the initiation of a genetic classification.

Authors:  Gert Van Goethem; Jean-Jacques Martin; Christine Van Broeckhoven
Journal:  Neuromolecular Med       Date:  2003       Impact factor: 3.843

Review 8.  Gastrointestinal and hepatic manifestations of mitochondrial disorders.

Authors:  Shamima Rahman
Journal:  J Inherit Metab Dis       Date:  2013-05-15       Impact factor: 4.982

9.  MPV17 Mutations Causing Adult-Onset Multisystemic Disorder With Multiple Mitochondrial DNA Deletions.

Authors:  Caterina Garone; Juan Carlos Rubio; Sarah E Calvo; Ali Naini; Kurenai Tanji; Salvatore Dimauro; Vamsi K Mootha; Michio Hirano
Journal:  Arch Neurol       Date:  2012-12

10.  Mutations in mitochondrial DNA polymerase-gamma promote breast tumorigenesis.

Authors:  Keshav K Singh; Vanniarajan Ayyasamy; Kjerstin M Owens; Manika Sapru Koul; Marija Vujcic
Journal:  J Hum Genet       Date:  2009-07-24       Impact factor: 3.172

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.