Literature DB >> 12638078

Lethal neonatal carnitine palmitoyltransferase II deficiency: an unusual presentation of a rare disorder.

Renu Sharma1, Anthony A Perszyk, Donald Marangi, Carmela Monteiro, Savithri Raja.   

Abstract

A term male newborn, appropriate for gestational age, developed hypothermia, severe cardiac dysrrhythmia, and nonoliguric hyperkalemia within 24 hours of birth. Despite the prenatal identification of cystic renal dysplasia without oligohydramnios, at birth, a solitary left leg vascular hemangioma and large palpable kidneys were the only anomalies. Gradually hypotonia, lethargy, and poor feeding developed and by 20 hours of age recurrent cardiac dysrrhythmias, myocardial dysfunction, and renal insufficiency with intermittent hyperkalemia were apparent. Episodes of apnea developed on day 7 followed by respiratory failure, recurrent cardiac dysrrhythmias, and death on day 12. Eventually laboratory and autopsy findings confirmed the diagnosis of lethal neonatal carnitine palmitoyltransferase II deficiency.

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Year:  2003        PMID: 12638078     DOI: 10.1055/s-2003-37952

Source DB:  PubMed          Journal:  Am J Perinatol        ISSN: 0735-1631            Impact factor:   1.862


  5 in total

1.  Congenital disorders of glycosylation type I: a rare but new cause of hyperechoic kidneys in infants and children due to early microcystic changes.

Authors:  Lucie Hertz-Pannier; Michele Déchaux; Martine Sinico; Sophie Emond; Valerie Cormier-Daire; Jean-Marie Saudubray; Francis Brunelle; Patrick Niaudet; Nathalie Seta; Pascale de Lonlay
Journal:  Pediatr Radiol       Date:  2005-11-22

2.  Neonatal carnitine palmitoyltransferase II deficiency: failure of treatment despite prolonged survival.

Authors:  Petra Hissink-Muller; Enrico Lopriore; Carolien Boelen; Frans Klumper; Marinus Duran; Frans Walther
Journal:  BMJ Case Rep       Date:  2009-06-26

3.  Renal mitochondrial cytopathies.

Authors:  Francesco Emma; Giovanni Montini; Leonardo Salviati; Carlo Dionisi-Vici
Journal:  Int J Nephrol       Date:  2011-07-27

4.  Infantile onset carnitine palmitoyltransferase 2 deficiency: Cortical polymicrogyria, schizencephaly, and gray matter heterotopias in an adolescent with normal development.

Authors:  Ivan Shelihan; Elsa Rossignol; Jean-Claude Décarie; Jean-Paul Bonnefont; Michèle Brivet; Catherine Brunel-Guitton; Grant A Mitchell
Journal:  JIMD Rep       Date:  2021-09-29

Review 5.  Carnitine supplementation for preterm infants with recurrent apnea.

Authors:  M Kumar; N S Kabra; B Paes
Journal:  Cochrane Database Syst Rev       Date:  2004-10-18
  5 in total

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