Literature DB >> 12493636

A prospective cross-sectional study of speech in patients with the 22q11 deletion syndrome.

Christina Persson1, Anette Lohmander, Radi Jönsson, Sólveig Oskarsdóttir, Ewa Söderpalm.   

Abstract

UNLABELLED: The purpose of this study was to investigate a consecutive series of 65 participants between 3 and 33 years of age (median age of 9 years and 4 months) with a confirmed 22q11.2 deletion, in order to ascertain the frequency and severity of articulation difficulties, velopharyngeal impairment (VPI), and the level of intelligibility. The majority had velopharyngeal impairment; over half of them to such a degree that surgery had been performed or was considered necessary. A high level of correct place and manner of consonants was only found in children with the 22q11 deletion syndrome from age 6. The most misarticulated consonants were stops and fricatives. Glottal articulation assessed in words and sentences was less frequent than expected according to earlier studies. A high prevalence of reduced intelligibility at different ages indicates an obvious communication limitation in younger children, and for some individuals even as teenagers and adults. EDUCATIONAL
OBJECTIVES: As a result of this activity, the participant will have knowledge about the frequency and severity of: (1) articulation difficulties; (2) velopharyngeal impairment; and (3) the level of intelligibility in patients with a 22q11.2 deletion.

Entities:  

Mesh:

Year:  2003        PMID: 12493636     DOI: 10.1016/s0021-9924(02)00133-8

Source DB:  PubMed          Journal:  J Commun Disord        ISSN: 0021-9924            Impact factor:   2.288


  10 in total

1.  Differences in the Tensor Veli Palatini Muscle and Hearing Status in Children With and Without 22q11.2 Deletion Syndrome.

Authors:  Jamie L Perry; Katelyn J Kotlarek; Kelly Spoloric; Adriane Baylis; Lakshmi Kollara; Jonathan M Grischkan; Richard Kirschner; David Gregory Bates; Mark Smith; Ursula Findlen
Journal:  Cleft Palate Craniofac J       Date:  2019-08-25

2.  Neuromotor deficits in children with the 22q11 deletion syndrome.

Authors:  Christina Sobin; Samantha H Monk; Karen Kiley-Brabeck; Jananne Khuri; Maria Karayiorgou
Journal:  Mov Disord       Date:  2006-12       Impact factor: 10.338

3.  Presenting phenotype in 100 children with the 22q11 deletion syndrome.

Authors:  Sólveig Oskarsdóttir; Christina Persson; Bengt O Eriksson; Anders Fasth
Journal:  Eur J Pediatr       Date:  2004-11-23       Impact factor: 3.183

4.  Factors affecting articulation skills in children with velocardiofacial syndrome and children with cleft palate or velopharyngeal dysfunction: a preliminary report.

Authors:  Adriane L Baylis; Benjamin Munson; Karlind T Moller
Journal:  Cleft Palate Craniofac J       Date:  2008-03

5.  The Oral Health of Patients with DiGeorge Syndrome (22q11) Microdeletion: A Case Report.

Authors:  Estephania Candelo; Maria Alejandra Estrada-Mesa; Adriana Jaramillo; Carlos Humberto Martinez-Cajas; Julio Cesar Osorio; Harry Pachajoa
Journal:  Appl Clin Genet       Date:  2021-06-01

6.  Frequency of 22q11.2 microdeletion in children with congenital heart defects in western poland.

Authors:  Anna Wozniak; Danuta Wolnik-Brzozowska; Marzena Wisniewska; Renata Glazar; Anna Materna-Kiryluk; Tomasz Moszura; Magdalena Badura-Stronka; Joanna Skolozdrzy; Maciej R Krawczynski; Joanna Zeyland; Waldemar Bobkowski; Ryszard Slomski; Anna Latos-Bielenska; Aldona Siwinska
Journal:  BMC Pediatr       Date:  2010-12-06       Impact factor: 2.125

7.  Self-reported speech problems in adolescents and young adults with 22q11.2 deletion syndrome: a cross-sectional cohort study.

Authors:  Nicole E Spruijt; Jacob As Vorstman; Moshe Kon; Aebele B Mink van der Molen
Journal:  Arch Plast Surg       Date:  2014-09-15

8.  Estimates of the Prevalence of Speech and Motor Speech Disorders in Youth With 22q11.2 Deletion Syndrome.

Authors:  Adriane L Baylis; Lawrence D Shriberg
Journal:  Am J Speech Lang Pathol       Date:  2019-02-21       Impact factor: 2.408

Review 9.  Speech-Language Disorders in 22q11.2 Deletion Syndrome: Best Practices for Diagnosis and Management.

Authors:  Cynthia B Solot; Debbie Sell; Anne Mayne; Adriane L Baylis; Christina Persson; Oksana Jackson; Donna M McDonald-McGinn
Journal:  Am J Speech Lang Pathol       Date:  2019-07-22       Impact factor: 4.018

10.  Consequences of rare diagnoses for education and daily life: development of an observation instrument.

Authors:  Gunilla Jaeger; AnnCatrin Röjvik; Erland Hjelmquist; André Hansla; Kerstin W Falkman
Journal:  Orphanet J Rare Dis       Date:  2022-04-12       Impact factor: 4.123

  10 in total

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