Literature DB >> 12483356

A case of I-cell disease (mucolipidosis II) presenting with craniosynostosis.

F Müjgan Aynaci1, Ertugrul Cakir, Osman Aynaci.   

Abstract

CASE REPORT: In this paper, a patient with mucolipidosis II (I-cell disease) is described. The initial findings were microcephaly and metopic craniosynostosis. He had coarse facial features and dysostosis multiplex. The first child in his family had died with severe bone pathology at 5 months of age.
CONCLUSION: The case is presented to emphasize that craniosynostosis may be the first symptom in mucolipidosis II.

Entities:  

Mesh:

Year:  2002        PMID: 12483356     DOI: 10.1007/s00381-002-0627-7

Source DB:  PubMed          Journal:  Childs Nerv Syst        ISSN: 0256-7040            Impact factor:   1.475


  8 in total

Review 1.  Lysosomal storage disorders in the newborn.

Authors:  Orna Staretz-Chacham; Tess C Lang; Mary E LaMarca; Donna Krasnewich; Ellen Sidransky
Journal:  Pediatrics       Date:  2009-04       Impact factor: 7.124

Review 2.  Radiological and clinical characterization of the lysosomal storage disorders: non-lipid disorders.

Authors:  E I Parker; M Xing; A Moreno-De-Luca; E Harmouche; M R Terk
Journal:  Br J Radiol       Date:  2013-11-14       Impact factor: 3.039

3.  Mucolipidosis Type II Secondary to GNPTAB Gene Deletion from India.

Authors:  Vykuntaraju K Gowda; Varun V Raghavan; Meenakshi Bhat; Asha Benakappa
Journal:  J Pediatr Neurosci       Date:  2017 Jan-Mar

4.  Case Report: Mucolipidosis II and III Alpha/Beta Caused by Pathogenic Variants in the GNPTAB Gene (Mucolipidosis).

Authors:  Shao-Jia Mao; Yu-Mei Zu; Yang-Li Dai; Chao-Chun Zou
Journal:  Front Pediatr       Date:  2022-04-08       Impact factor: 3.418

5.  Craniosynostosis in a child with I-cell disease: The need for genetic analysis before contemplating surgery in craniosynostosis.

Authors:  Lakshmanarao Chittem; Suchanda Bhattacharjee; Prajnya Ranganath
Journal:  J Pediatr Neurosci       Date:  2014-01

6.  A case of I-cell disease (mucolipidosis II) presenting with short femurs on prenatal ultrasound and profound diaphyseal cloaking.

Authors:  Thomas Capobres; Gauravi Sabharwal; Brent Griffith
Journal:  BJR Case Rep       Date:  2016-07-28

7.  GNPTAB c.2404C > T nonsense mutation in a patient with mucolipidosis III alpha/beta: a case report.

Authors:  Chi-Chun Ho; Lilian Li-Yan Tsung; Kam-Tim Liu; Wing-Tat Poon
Journal:  BMC Med Genet       Date:  2018-09-12       Impact factor: 2.103

8.  Mucolipidosis II: first report from Saudi Arabia.

Authors:  Majid Alfadhel; Wafaa AlShehhi; Hesham Alshaalan; Mohammed Al Balwi; Wafaa Eyaid; Wafaa Eyaida
Journal:  Ann Saudi Med       Date:  2013 Jul-Aug       Impact factor: 1.526

  8 in total

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