Literature DB >> 12131731

Irreducible thoracic spondyloptosis in a child with neurofibromatosis: a rationale for treatment.

B Guirguis Hanna1, Stephan G Pill, Denis S Drummond.   

Abstract

STUDY
DESIGN: A case report and review of literature are presented.
OBJECTIVES: To describe the surgical management of a midthoracic spondyloptosis associated with kyphosis in a child with neurofibromatosis, an extremely rare but a potentially high-morbidity complication. SUMMARY OF BACKGROUND DATA: Dystrophic kyphoscoliotic spinal deformity is the most common orthopedic sequela of neurofibromatosis. Spondyloptosis is a rare complication but with the potential for high morbidity if the diagnosis is missed or undertreated. Reported cases are rare.
METHODS: A severe thoracic spondyloptosis occurred in a 7-year-old girl with peripheral neurofibromatosis who presented with transient paraparesis after a fall. The kyphosis was reduced by cantilever correction forces, achieving side-to-side (bayonet) apposition rather than anatomic reduction of the spondyloptosis. This was followed by anterior spinal arthrodesis and structural grafting.
RESULTS: Two and a half years after the surgery there is no loss of correction, and the patient has remained neurologically recovered.
CONCLUSIONS: Posterior correction of the gibbus in a bayonet apposition and stabilization with a two-rod construct followed by anterior spinal arthrodesis and structural grafting seem to offer efficient surgical treatment.

Entities:  

Mesh:

Year:  2002        PMID: 12131731     DOI: 10.1097/00007632-200207150-00022

Source DB:  PubMed          Journal:  Spine (Phila Pa 1976)        ISSN: 0362-2436            Impact factor:   3.468


  3 in total

1.  Dystrophic thoracic spine dislocation associated with type-1 neurofibromatosis: Case report and rationale for treatment.

Authors:  David Meneses-Quintero; Fernando Alvarado-Gómez; Gabriel Alcalá-Cerra
Journal:  J Craniovertebr Junction Spine       Date:  2015 Apr-Jun

Review 2.  Spontaneous rotational dislocation of the lumbar spine in type 1 neurofibromatosis: A case report and literature review.

Authors:  Fei Jia; Xingang Cui; Guodong Wang; Xiaoyang Liu; Jianmin Sun
Journal:  Medicine (Baltimore)       Date:  2019-04       Impact factor: 1.817

3.  Rotatory Dislocation of the Spine in Dystrophic Kyphoscoliosis Secondary to Neurofibromatosis Type 1.

Authors:  Athanasios I Tsirikos; Rakesh Dhokia; Sarah Wordie
Journal:  J Cent Nerv Syst Dis       Date:  2018-12-18
  3 in total

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