Literature DB >> 12119817

Oral self-mutilation in the Lesch-Nyhan syndrome.

Jae-Ho Lee1, Robert J Berkowitz, Byung-Jai Choi.   

Abstract

Lesch-Nyhan Syndrome is a disorder caused by congenital absence of a purine metabolic enzyme, hypoxanthine-guanine phosphoribosyl transferase (HPRT). This syndrome is characterized clinically by mental retardation, chorea, athetosis, hyperuricemia, uricosuria and self-mutilation. This report is of two children, who are cousins, both of whom have Lesch-Nyhan syndrome and presented with severe self-mutilation wounds on their lip(s). Vital pulpotomy and coronal resection was done as a more conservative approach than extracting all offending teeth. By maintaining the root portion of the teeth in the bone, it is expected that preservation of the alveolar bone will be achieved.

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Year:  2002        PMID: 12119817

Source DB:  PubMed          Journal:  ASDC J Dent Child        ISSN: 1945-1954


  5 in total

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5.  Autoextraction of Permanent Incisors and Self-Inflicted Orodental Trauma in a Severely Burned Child.

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  5 in total

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