Literature DB >> 12107816

WFS1 mutations in Spanish patients with diabetes mellitus and deafness.

Enric Domènech1, Montse Gómez-Zaera, Virginia Nunes.   

Abstract

Wolfram syndrome (WS) is an autosomal recessive neurodegenerative disorder characterised by early onset diabetes mellitus and progressive optic atrophy, as well as other clinical features such as deafness, diabetes insipida, renal tract abnormalities and diverse psychiatric illnesses. A gene responsible for WS was identified in 4p16.1 (WFS1). It encodes a putative 890 amino acid transmembrane protein expressed in a wide spectrum of tissues. Recently, a new locus for WS has been located on 4q22-24, providing additional evidence for the genetic heterogeneity of this syndrome. We have studied the presence of WFS1 variants in three groups of individuals: patients with diabetes mellitus, patients with deafness and patients with both conditions. A fourth group of healthy subjects was used as control. We have identified a total of 18 nucleotide changes in the WFS1 gene: three mutations and 15 polymorphisms. Six of these changes were previously undescribed. Four of the 15 polymorphisms studied among the patients group present statistical differences in the allelic and genotypic distribution when comparing affected vs control groups.

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Year:  2002        PMID: 12107816     DOI: 10.1038/sj.ejhg.5200823

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  9 in total

1.  Clinical application of a custom AmpliSeq library and ion torrent PGM sequencing to comprehensive mutation screening for deafness genes.

Authors:  Shin-Ya Nishio; Yoshiharu Hayashi; Manabu Watanabe; Shin-Ichi Usami
Journal:  Genet Test Mol Biomarkers       Date:  2015-01-14

Review 2.  Nuclear membrane diversity: underlying tissue-specific pathologies in disease?

Authors:  Howard J Worman; Eric C Schirmer
Journal:  Curr Opin Cell Biol       Date:  2015-06-24       Impact factor: 8.382

3.  Impact of polymorphisms in WFS1 on prediabetic phenotypes in a population-based sample of middle-aged people with normal and abnormal glucose regulation.

Authors:  T Sparsø; G Andersen; A Albrechtsen; T Jørgensen; K Borch-Johnsen; A Sandbaek; T Lauritzen; J Wasson; M A Permutt; B Glaser; S Madsbad; O Pedersen; T Hansen
Journal:  Diabetologia       Date:  2008-06-21       Impact factor: 10.122

4.  Autoimmune disease in a DFNA6/14/38 family carrying a novel missense mutation in WFS1.

Authors:  Michael S Hildebrand; Jessica L Sorensen; Maren Jensen; William J Kimberling; Richard J H Smith
Journal:  Am J Med Genet A       Date:  2008-09-01       Impact factor: 2.802

5.  Several novel nuclear envelope transmembrane proteins identified in skeletal muscle have cytoskeletal associations.

Authors:  Gavin S Wilkie; Nadia Korfali; Selene K Swanson; Poonam Malik; Vlastimil Srsen; Dzmitry G Batrakou; Jose de las Heras; Nikolaj Zuleger; Alastair R W Kerr; Laurence Florens; Eric C Schirmer
Journal:  Mol Cell Proteomics       Date:  2010-09-27       Impact factor: 5.911

6.  Wolfram syndrome: new mutations, different phenotype.

Authors:  Concetta Aloi; Alessandro Salina; Lorenzo Pasquali; Francesca Lugani; Katia Perri; Chiara Russo; Ramona Tallone; Gian Marco Ghiggeri; Renata Lorini; Giuseppe d'Annunzio
Journal:  PLoS One       Date:  2012-01-04       Impact factor: 3.240

7.  WFS1 mutation screening in a large series of Japanese hearing loss patients: Massively parallel DNA sequencing-based analysis.

Authors:  Masafumi Kobayashi; Maiko Miyagawa; Shin-Ya Nishio; Hideaki Moteki; Taro Fujikawa; Kenji Ohyama; Hirofumi Sakaguchi; Ikuyo Miyanohara; Akiko Sugaya; Yasushi Naito; Shin-Ya Morita; Yukihiko Kanda; Masahiro Takahashi; Kotaro Ishikawa; Yuki Nagano; Tetsuya Tono; Chie Oshikawa; Chiharu Kihara; Haruo Takahashi; Yoshihiro Noguchi; Shin-Ichi Usami
Journal:  PLoS One       Date:  2018-03-12       Impact factor: 3.240

Review 8.  Tissue specificity in the nuclear envelope supports its functional complexity.

Authors:  Jose I de Las Heras; Peter Meinke; Dzmitry G Batrakou; Vlastimil Srsen; Nikolaj Zuleger; Alastair Rw Kerr; Eric C Schirmer
Journal:  Nucleus       Date:  2013-11-08       Impact factor: 4.197

Review 9.  A polygenic score for schizophrenia predicts glycemic control.

Authors:  Han Cao; Junfang Chen; Andreas Meyer-Lindenberg; Emanuel Schwarz
Journal:  Transl Psychiatry       Date:  2017-12-18       Impact factor: 6.222

  9 in total

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