Literature DB >> 12064861

Hemochromatosis and porphyria.

Richard W Lambrecht1, Herbert L Bonkovsky.   

Abstract

A 52-year-old man presented to his primary care physician with blisters and sores on the backs of his hands. Laboratory studies supported a diagnosis of porphyria cutanea tarda, complicated by the presence of both the C282Y and H63D mutations in the HFE gene, with susequent iron over-load. This case illustrates the need to understand the pathogenesis of porphyria cutanea tarda, particularly the role of excess iron in the overproduction of uroporphyrin. Iron, by catalyzing the formation of reactive oxygen species, can enhance uroporphyrin formation by increasing the rate at which uroporphyrinogen is oxidized to urophophyrin. Iron may also act indirectly to inhibit uroporphyrinogen decarboxylase activity by enhancing the formation of non-porphyrin products of porphyrinogen oxidation that are themselves direct inhibitors of the enzyme. Finally, iron can act to increase urophorphyrin production by inducing delta-aminolevulinic acid synthase, thus increasing the amount of delta-aminolevulinic acid, the precursor to uroporphyrinogen, present in the cell. After the diagnosis, the patient underwent an aggressive series of therapeutic phlebotomies to reduce iron levels, and gradually the cutaneous manifestations of porphyria cutanea tarda improved.

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Year:  2002        PMID: 12064861

Source DB:  PubMed          Journal:  Semin Gastrointest Dis        ISSN: 1049-5118


  4 in total

1.  Effects of a single dose of oral iron on hepcidin concentrations in human urine and serum analyzed by a robust LC-MS/MS method.

Authors:  Sun-Il Hwang; Yong-Yook Lee; Jung-Ok Park; H James Norton; Elene Clemens; Laura W Schrum; Herbert L Bonkovsky
Journal:  Clin Chim Acta       Date:  2011-08-16       Impact factor: 3.786

Review 2.  HFE gene in primary and secondary hepatic iron overload.

Authors:  Giada Sebastiani; Ann-P Walker
Journal:  World J Gastroenterol       Date:  2007-09-21       Impact factor: 5.742

3.  Facial hyperpigmentation and crusted papules on the hands.

Authors:  Audrey C Leasure; Noel Turner; Ilya Lim
Journal:  JAAD Case Rep       Date:  2021-11-19

4.  Primary hemochromatosis presented by porphyria cutanea tarda: a case report.

Authors:  H Jorn Bovenschen; Wynand H P M Vissers
Journal:  Cases J       Date:  2009-06-17
  4 in total

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