Literature DB >> 11982770

Clinical and molecular diagnostic criteria of congenital atrichia with papular lesions.

Abraham Zlotogorski1, Andrei A Panteleyev, Vincent M Aita, Angela M Christiano.   

Abstract

Congenital atrichia with papular lesions is a rare, autosomal recessive form of total alopecia and mutations in the hairless (hr) gene have been implicated in this disorder. Published estimates of the prevalence of this disorder remain surprisingly low considering pathogenetic mutations in hr have been found in distinct populations around the world. Therefore, it is likely that congenital atrichia with papular lesions is more common than previously thought and is often mistaken for the putative autoimmune form of alopecia universalis. To clarify this discrepancy, we propose criteria for the clinical diagnosis of congenital atrichia with papular lesions. Among these is the novel report of the consistent observation of hypopigmented whitish streaks on the scalp surface of affected individuals. Additionally, we report the identification of a novel missense mutation in hr from a family of Arab Palestinian origin that exhibits the pathognomonic features of atrichia with papular lesions. Collectively, we anticipate that an increased recognition of this disorder will result in more accurate diagnosis and the sparing of unnecessarily treatment to patients.

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Year:  2002        PMID: 11982770     DOI: 10.1046/j.1523-1747.2001.01767.x

Source DB:  PubMed          Journal:  J Invest Dermatol        ISSN: 0022-202X            Impact factor:   8.551


  17 in total

Review 1.  [Genetically induced hair diseases].

Authors:  T Wiederholt; P Poblete-Gutiérrez; J Frank
Journal:  Hautarzt       Date:  2003-07-04       Impact factor: 0.751

2.  Atrichia with Papular Lesions: Importance of Histology at an Early Disease Stage.

Authors:  Vanessa B Rocha; Nilceo Michalany; Neusa Y S Valente; Luciana B Pereira; Aline Donati
Journal:  Skin Appendage Disord       Date:  2017-09-28

3.  Detection of a novel missense mutations in atrichia with papular lesions.

Authors:  Deborah Lee; Sang-Hyun Kim; Ji-Sung Chun; Myeong-Hoon Joo; Ji-Yeon Kim; Seon-Wook Hwang; Hyo-Joon Kang; Sung-Wook Park; Ho-Suk Sung
Journal:  Ann Dermatol       Date:  2011-05-27       Impact factor: 1.444

Review 4.  The role of vitamin D receptor mutations in the development of alopecia.

Authors:  Peter J Malloy; David Feldman
Journal:  Mol Cell Endocrinol       Date:  2011-06-13       Impact factor: 4.102

5.  Atrichia with papular lesions.

Authors:  Manish Bansal; Kajal Manchanda; Sachin Lamba; Ss Pandey
Journal:  Int J Trichology       Date:  2011-07

6.  Analysis of hairless corepressor mutants to characterize molecular cooperation with the vitamin D receptor in promoting the mammalian hair cycle.

Authors:  Jui-Cheng Hsieh; Stephanie A Slater; G Kerr Whitfield; Jamie L Dawson; Grace Hsieh; Craig Sheedy; Carol A Haussler; Mark R Haussler
Journal:  J Cell Biochem       Date:  2010-06-01       Impact factor: 4.429

7.  Photoletter to the editor: Congenital atrichia associated with an uncommon mutation of HR gene.

Authors:  Ana Pedrosa; Ana Nogueira; Paulo Morais; Ana Filipa Duarte; Joana Pardal; Alberto Mota; Filomena Azevedo
Journal:  J Dermatol Case Rep       Date:  2013-03-30

8.  Mutations in the hairless gene underlie APL in three families of Pakistani origin.

Authors:  Liv Kraemer; Muhammad Wajid; Yutaka Shimomura; Angela M Christiano
Journal:  J Dermatol Sci       Date:  2008-04       Impact factor: 4.563

9.  Founder mutations in the lipase h gene in families with autosomal recessive woolly hair/hypotrichosis.

Authors:  Yutaka Shimomura; Muhammad Wajid; Abraham Zlotogorski; Young-Jin Lee; Robert H Rice; Angela M Christiano
Journal:  J Invest Dermatol       Date:  2009-03-05       Impact factor: 8.551

10.  Ligand-independent regulation of the hairless promoter by vitamin D receptor.

Authors:  Andrew Engelhard; Robert C Bauer; Alexandre Casta; Karima Djabali; Angela M Christiano
Journal:  Photochem Photobiol       Date:  2008-02-07       Impact factor: 3.421

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