Literature DB >> 11829484

Identification of a mutation causing mucopolysaccharidosis type IIIA in New Zealand Huntaway dogs.

Gouri Yogalingam1, Tony Pollard, Briony Gliddon, Robert D Jolly, John J Hopwood.   

Abstract

Mucopolysaccharidosis type IIIA (MPS IIIA) is an autosomal recessive disease that occurs due to a deficiency of heparan sulfate sulfamidase (SGSH). The deficiency of SGSH results in the lysosomal accumulation and urinary excretion of the glycosaminoglycan heparan sulfate. The clinical severity of MPS IIIA is predominantly characterized by severe central nervous system degeneration. Naturally occurring MPS IIIA has recently been described in New Zealand Huntaway dogs, with similar disease progression and biochemical characteristics observed in severely affected MPS IIIA patients. Here, we identify the disease-causing mutation in the MPS IIIA Huntaway dog as 708-709insC. The frequency of the 708-709insC mutation in a sample group of 203 New Zealand Huntaway dogs was determined to be 3.8%. The identification of the 708-709insC mutation will permit the identification of heterozygous carriers as an initial step toward establishing a breeding colony of MPS IIIA dogs for the study of various therapeutic strategies targeted to the central nervous system.

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Year:  2002        PMID: 11829484     DOI: 10.1006/geno.2002.6699

Source DB:  PubMed          Journal:  Genomics        ISSN: 0888-7543            Impact factor:   5.736


  14 in total

1.  Evaluation of Disease Lesions in the Developing Canine MPS IIIA Brain.

Authors:  Leanne K Winner; Neil R Marshall; Robert D Jolly; Paul J Trim; Stephen K Duplock; Marten F Snel; Kim M Hemsley
Journal:  JIMD Rep       Date:  2018-06-20

2.  Evaluation of enzyme dose and dose-frequency in ameliorating substrate accumulation in MPS IIIA Huntaway dog brain.

Authors:  Barbara King; Neil Marshall; Helen Beard; Sofia Hassiotis; Paul J Trim; Marten F Snel; Tina Rozaklis; Robert D Jolly; John J Hopwood; Kim M Hemsley
Journal:  J Inherit Metab Dis       Date:  2014-11-25       Impact factor: 4.982

3.  Slow, continuous enzyme replacement via spinal CSF in dogs with the paediatric-onset neurodegenerative disease, MPS IIIA.

Authors:  Barbara King; Neil R Marshall; Sofia Hassiotis; Paul J Trim; Justin Tucker; Kathryn Hattersley; Marten F Snel; Robert D Jolly; John J Hopwood; Kim M Hemsley
Journal:  J Inherit Metab Dis       Date:  2016-11-10       Impact factor: 4.982

4.  A model of mucopolysaccharidosis IIIB (Sanfilippo syndrome type IIIB): N-acetyl-alpha-D-glucosaminidase deficiency in Schipperke dogs.

Authors:  N M Ellinwood; P Wang; T Skeen; N J H Sharp; M Cesta; S Decker; N J Edwards; I Bublot; J N Thompson; W Bush; E Hardam; M E Haskins; U Giger
Journal:  J Inherit Metab Dis       Date:  2003       Impact factor: 4.982

Review 5.  Animal models for mucopolysaccharidosis disorders and their clinical relevance.

Authors:  Mark E Haskins
Journal:  Acta Paediatr       Date:  2007-04       Impact factor: 2.299

Review 6.  Pathogenesis and treatment of spine disease in the mucopolysaccharidoses.

Authors:  Sun H Peck; Margret L Casal; Neil R Malhotra; Can Ficicioglu; Lachlan J Smith
Journal:  Mol Genet Metab       Date:  2016-06-04       Impact factor: 4.797

7.  Lentiviral-mediated gene correction of mucopolysaccharidosis type IIIA.

Authors:  Donald S Anson; Chantelle McIntyre; Belinda Thomas; Rachel Koldej; Enzo Ranieri; Ainslie Roberts; Peter R Clements; Kylie Dunning; Sharon Byers
Journal:  Genet Vaccines Ther       Date:  2007-01-16

8.  Progressive neurologic and somatic disease in a novel mouse model of human mucopolysaccharidosis type IIIC.

Authors:  Sara Marcó; Anna Pujol; Carles Roca; Sandra Motas; Albert Ribera; Miguel Garcia; Maria Molas; Pilar Villacampa; Cristian S Melia; Víctor Sánchez; Xavier Sánchez; Joan Bertolin; Jesús Ruberte; Virginia Haurigot; Fatima Bosch
Journal:  Dis Model Mech       Date:  2016-08-04       Impact factor: 5.758

9.  An Engineered sgsh Mutant Zebrafish Recapitulates Molecular and Behavioural Pathobiology of Sanfilippo Syndrome A/MPS IIIA.

Authors:  Alon M Douek; Mitra Amiri Khabooshan; Jason Henry; Sebastian-Alexander Stamatis; Florian Kreuder; Georg Ramm; Minna-Liisa Änkö; Donald Wlodkowic; Jan Kaslin
Journal:  Int J Mol Sci       Date:  2021-05-31       Impact factor: 5.923

Review 10.  DNA testing in neurologic diseases.

Authors:  D P O'Brien; T Leeb
Journal:  J Vet Intern Med       Date:  2014-06-24       Impact factor: 3.333

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