Literature DB >> 11704046

Lens changes in hereditary hyperferritinemia-cataract syndrome.

A Chang-Godinich1, S Ades, D Schenkein, D Brooks, D Stambolian, M B Raizman.   

Abstract

PURPOSE: To provide detailed description and illustration of the lens changes found in hereditary hyperferritinemia-cataract syndrome, a newly reported autosomal dominant condition.
METHODS: Observational case reports. A 19-year-old man was referred for evaluation of possible hereditary hyperferritinemia-cataract syndrome. His serum ferritin level was increased at 1291 microg/L during a routine screening examination. Genetic analysis revealed mutation G51C on chromosome 19, predicting an altered iron response element in L-ferritin mRNA. Subsequent evaluation of his 46-year-old father revealed similar findings.
RESULTS: Multiple breadcrumb-like nuclear and cortical lens opacities were seen in this father-son pair. These cases represent the first detailed description and illustration of hereditary hyperferritinemia-cataract syndrome cataracts in the ophthalmic literature.
CONCLUSION: Hereditary hyperferritinemia-cataract syndrome can be associated with distinct breadcrumb-like lens opacities. Recognition of these characteristic cataracts may aid identification and study of patients with this unusual disorder and provide insight into mechanisms of cataract formation.

Entities:  

Mesh:

Substances:

Year:  2001        PMID: 11704046     DOI: 10.1016/s0002-9394(01)01106-0

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  2 in total

Review 1.  Recent advance in molecular iron metabolism: translational disorders of ferritin.

Authors:  Junji Kato; Yoshiro Niitsu
Journal:  Int J Hematol       Date:  2002-10       Impact factor: 2.490

2.  Homozygous mutation of the 5'UTR region of the L-Ferritin gene in the hereditary hyperferritinemia cataract syndrome and its impact on the phenotype.

Authors:  Muriel Giansily-Blaizot; Séverine Cunat; Grégory Moulis; Jean-François Schved; Patricia Aguilar-Martinez
Journal:  Haematologica       Date:  2013-01-08       Impact factor: 9.941

  2 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.