Literature DB >> 11598576

Oral and craniofacial findings in Fabry's disease: a report of 13 patients.

L Baccaglini1, R Schiffmann, M T Brennan, H E Lancaster, A B Kulkarni, J S Brahim.   

Abstract

OBJECTIVE: Fabry's disease is an X-linked metabolic disease caused by the deficiency of the lysosomal enzyme alpha-galactosidase A. The purpose of this study was to assess oral and craniofacial findings in a cohort of patients with Fabry's disease to facilitate recognition of this condition and early treatment of its manifestations. STUDY
DESIGN: This is a case series describing oral and craniofacial findings of 13 male patients diagnosed with Fabry's disease. Data were collected by means of a standardized questionnaire, clinical examination, panoramic and cephalometric radiographs, and magnetic resonance imaging.
RESULTS: A variety of abnormalities are described, including an increased prevalence of cysts/pseudocysts of the maxillary sinuses (PCMs) and the presence of maxillary prognathism.
CONCLUSION: Given the high prevalence of oral and dental abnormalities, we recommend a thorough stomatologic evaluation of these patients.

Entities:  

Mesh:

Year:  2001        PMID: 11598576     DOI: 10.1067/moe.2001.114833

Source DB:  PubMed          Journal:  Oral Surg Oral Med Oral Pathol Oral Radiol Endod        ISSN: 1079-2104


  4 in total

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Journal:  Lasers Med Sci       Date:  2007-12-05       Impact factor: 3.161

2.  A case of angiokeratoma circumscriptum of the tongue: response with carbon dioxide and pulsed dye laser.

Authors:  Hemanta Kumar Kar; Lipy Gupta
Journal:  J Cutan Aesthet Surg       Date:  2011-09

Review 3.  Genetic background of supernumerary teeth.

Authors:  Aslı Subasioglu; Selcuk Savas; Ebru Kucukyilmaz; Servet Kesim; Ahmet Yagci; Munis Dundar
Journal:  Eur J Dent       Date:  2015 Jan-Mar

4.  Life-threatening bleeding from gastric mucosal angiokeratomas during anticoagulation: A case report of Fabry disease.

Authors:  Eungu Kang; Yoon-Myung Kim; Dae-Hee Kim; Han-Wook Yoo; Beom Hee Lee
Journal:  Medicine (Baltimore)       Date:  2017-02       Impact factor: 1.889

  4 in total

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