Literature DB >> 11384588

Dominant radial drusen and Arg345Trp EFEMP1 mutation.

M Matsumoto1, E I Traboulsi.   

Abstract

PURPOSE: To report a new North American family with dominant radial drusen and Arg345Trp mutation in the EFEMP1 gene.
METHODS: Clinical and molecular genetic family study.
RESULTS: Four family members had macular drusen, and one had submacular fibrosis and visual loss. An Arg345Trp mutation of the EFEMP1 gene was detected in three affected family members, but not in three unaffected members.
CONCLUSION: The Arg345Trp mutation remains the only cause of Doyne hereditary macular dystrophy, also known as Malattia Leventinese or radial dominant drusen.

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Year:  2001        PMID: 11384588     DOI: 10.1016/s0002-9394(00)00926-0

Source DB:  PubMed          Journal:  Am J Ophthalmol        ISSN: 0002-9394            Impact factor:   5.258


  6 in total

1.  Multimodal morphological and functional characterization of Malattia Leventinese.

Authors:  Giuseppe Querques; Benjamin Guigui; Nicolas Leveziel; Lea Querques; Francesco Bandello; Eric H Souied
Journal:  Graefes Arch Clin Exp Ophthalmol       Date:  2012-07-20       Impact factor: 3.117

2.  Indocyanine green angiography features of Malattia leventinese.

Authors:  E H Souied; N Leveziel; G Querques; J Darmon; G Coscas; G Soubrane
Journal:  Br J Ophthalmol       Date:  2006-03       Impact factor: 4.638

3.  A novel haplotype with the R345W mutation in the EFEMP1 gene associated with autosomal dominant drusen in a Japanese family.

Authors:  Tomokazu Takeuchi; Takaaki Hayashi; Matthew Bedell; Kang Zhang; Hisashi Yamada; Hiroshi Tsuneoka
Journal:  Invest Ophthalmol Vis Sci       Date:  2009-10-22       Impact factor: 4.799

4.  Exome Sequencing Identifies a Missense Variant in EFEMP1 Co-Segregating in a Family with Autosomal Dominant Primary Open-Angle Glaucoma.

Authors:  Donna S Mackay; Thomas M Bennett; Alan Shiels
Journal:  PLoS One       Date:  2015-07-10       Impact factor: 3.240

5.  Diagnostic definition of malattia leventinese in a family from Colombia

Authors:  Nancy Gelvez; Paula Hurtado-Villa; Silvia Flórez; Anne Charlotte Brieke; Francisco Rodríguez; Ana María Bertolotto; Martha L Tamayo
Journal:  Biomedica       Date:  2021-09-22       Impact factor: 0.935

6.  First reported case of Doyne honeycomb retinal dystrophy (Malattia Leventinese/autosomal dominant drusen) in Scandinavia.

Authors:  Inger Norlyk Sheyanth; Ihab Bishara Lolas; Henrik Okkels; Ligor Pradeep Kiruparajan; Søren Kromann Abildgaard; Michael Bjørn Petersen
Journal:  Mol Genet Genomic Med       Date:  2021-03-10       Impact factor: 2.183

  6 in total

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