Literature DB >> 11348474

Novel keratin 17 mutations in pachyonychia congenita type 2.

F J Smith1, C M Coleman, N M Bayoumy, R Tenconi, J Nelson, A David, W H McLean.   

Abstract

Pachyonychia congenita type 2 is an inherited ectodermal dysplasia characterized by hypertrophic nail dystrophy and multiple pilosebaceous cysts. Focal nonepidermolytic palmoplantar keratoderma, natal teeth, and pili torti may also be present. Epithelial tissues affected in pachyonychia congenita type 2 express the keratin pair K6b/K17. Here, we report three novel heterozygous mutations in the K17 gene (KRT17A) in patients presenting with pachyonychia congenita type 2. These mutations, R94-98del (deletion of the peptide sequence RLASY) and missense mutations R94P and L95Q, are all within the 1A domain hotspot for pathogenic keratin mutations.

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Year:  2001        PMID: 11348474     DOI: 10.1046/j.1523-1747.2001.01335.x

Source DB:  PubMed          Journal:  J Invest Dermatol        ISSN: 0022-202X            Impact factor:   8.551


  3 in total

1.  KERATIN 17-related recessive atypical pachyonychia congenita with variable hair and tooth anomalies.

Authors:  Mine Koprulu; Muhammad Naeem; Gökhan Nalbant; Rana M Kamran Shabbir; Tariq Mahmood; Zele Huma; Sajid Malik; Aslıhan Tolun
Journal:  Eur J Hum Genet       Date:  2022-06-09       Impact factor: 4.246

2.  Pachyonychia congenita type 2, N92S mutation of keratin 17 gene: clinical features, mutation analysis and pathological view.

Authors:  Ozgur Cogulu; Huseyin Onay; Ayca Aykut; Neil J Wilson; Frances J D Smith; Tugrul Dereli; Ferda Ozkinay
Journal:  Eur J Pediatr       Date:  2008-12-24       Impact factor: 3.183

3.  Keratin 17 null mice exhibit age- and strain-dependent alopecia.

Authors:  Kevin M McGowan; Xuemei Tong; Emma Colucci-Guyon; Francina Langa; Charles Babinet; Pierre A Coulombe
Journal:  Genes Dev       Date:  2002-06-01       Impact factor: 11.361

  3 in total

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