Literature DB >> 11339376

Taking advantage of early diagnosis: preschool children with the 22q11.2 deletion.

M Gerdes1, C Solot, P P Wang, D M McDonald-McGinn, E H Zackai.   

Abstract

PURPOSE: The purpose of this study is to review the neurodevelopmental outcome of infants and preschoolers with a 22q11.2 microdeletion and to discuss the our clinical observations of clinical implications for educational and therapeutic interventions.
METHODS: One hundred twelve children (4 to 70 mos) with the 22q11.2 deletion were assessed using standardized tests (Bayley Scales of Infant Development-II, Preschool Language Scales, Wechsler Preschool and Primary Scales of Intelligence-Revised).
RESULTS: Fifty-four percent of the children were significantly delayed, 24% had mild delay, 22% had average cognitive development, and 80% were below average in language development. Delays are not explained by cardiac defects or palatal defects.
CONCLUSION: Developmental delays, mild hypotonia, language and speech delays, and feeding disorders are common, and this finding indicates the need for early intervention services beginning in infancy for children with the 22q11.2 deletion.

Entities:  

Mesh:

Year:  2001        PMID: 11339376     DOI: 10.1097/00125817-200101000-00009

Source DB:  PubMed          Journal:  Genet Med        ISSN: 1098-3600            Impact factor:   8.822


  17 in total

1.  22q11.2 deletion syndrome: are motor deficits more than expected for IQ level?

Authors:  Nancy J Roizen; Anne M Higgins; Kevin M Antshel; Wanda Fremont; Robert Shprintzen; Wendy R Kates
Journal:  J Pediatr       Date:  2010-06-19       Impact factor: 4.406

2.  Early language measures associated with later psychosis features in 22q11.2 deletion syndrome.

Authors:  Cynthia B Solot; Tyler M Moore; Terrence Blaine Crowley; Marsha Gerdes; Edward Moss; Daniel E McGinn; Beverly S Emanuel; Elaine H Zackai; Sean Gallagher; Monica E Calkins; Kosha Ruparel; Ruben C Gur; Donna M McDonald-McGinn; Raquel E Gur
Journal:  Am J Med Genet B Neuropsychiatr Genet       Date:  2020-07-27       Impact factor: 3.568

Review 3.  Developmental Support for Infants With Genetic Disorders.

Authors:  Monica H Wojcik; Jane E Stewart; Susan E Waisbren; Jonathan S Litt
Journal:  Pediatrics       Date:  2020-05       Impact factor: 7.124

Review 4.  A review of neurocognitive and behavioral profiles associated with 22q11 deletion syndrome: implications for clinical evaluation and treatment.

Authors:  Opal Ousley; Kimberly Rockers; Mary Lynn Dell; Karlene Coleman; Joseph F Cubells
Journal:  Curr Psychiatry Rep       Date:  2007-04       Impact factor: 5.285

5.  Assessment of parental disclosure of a 22q11.2 deletion syndrome diagnosis and implications for clinicians.

Authors:  Dana Faux; Kelly Schoch; Sonja Eubanks; Stephen R Hooper; Vandana Shashi
Journal:  J Genet Couns       Date:  2012-08-31       Impact factor: 2.537

Review 6.  Cognitive, behavioural and psychiatric phenotype in 22q11.2 deletion syndrome.

Authors:  Nicole Philip; Anne Bassett
Journal:  Behav Genet       Date:  2011-05-15       Impact factor: 2.805

7.  Elucidating the diagnostic odyssey of 22q11.2 deletion syndrome.

Authors:  Lisa D Palmer; Nancy J Butcher; Erik Boot; Kathleen A Hodgkinson; Tracy Heung; Eva W C Chow; Alina Guna; T Blaine Crowley; Elaine Zackai; Donna M McDonald-McGinn; Anne S Bassett
Journal:  Am J Med Genet A       Date:  2018-04       Impact factor: 2.802

Review 8.  Modeling a model: Mouse genetics, 22q11.2 Deletion Syndrome, and disorders of cortical circuit development.

Authors:  Daniel W Meechan; Thomas M Maynard; Eric S Tucker; Alejandra Fernandez; Beverly A Karpinski; Lawrence A Rothblat; Anthony-S LaMantia
Journal:  Prog Neurobiol       Date:  2015-04-09       Impact factor: 11.685

Review 9.  Practical guidelines for managing adults with 22q11.2 deletion syndrome.

Authors:  Wai Lun Alan Fung; Nancy J Butcher; Gregory Costain; Danielle M Andrade; Erik Boot; Eva W C Chow; Brian Chung; Cheryl Cytrynbaum; Hanna Faghfoury; Leona Fishman; Sixto García-Miñaúr; Susan George; Anthony E Lang; Gabriela Repetto; Andrea Shugar; Candice Silversides; Ann Swillen; Therese van Amelsvoort; Donna M McDonald-McGinn; Anne S Bassett
Journal:  Genet Med       Date:  2015-01-08       Impact factor: 8.822

10.  Frequency and clinical manifestations of patients with primary immunodeficiency disorders in Iran: update from the Iranian Primary Immunodeficiency Registry.

Authors:  Nima Rezaei; Asghar Aghamohammadi; Mostafa Moin; Zahra Pourpak; Masoud Movahedi; Mohammad Gharagozlou; Lida Atarod; Bahram Mirsaeid Ghazi; Anna Isaeian; Maryam Mahmoudi; Kamran Abolmaali; Davoud Mansouri; Saba Arshi; Naser Javaher Tarash; Roya Sherkat; Hedayat Akbari; Reza Amin; Abdolvahab Alborzi; Sara Kashef; Reza Farid; Iraj Mohammadzadeh; Mehrnaz Sadeghi Shabestari; Mohammad Nabavi; Abolhassan Farhoudi
Journal:  J Clin Immunol       Date:  2006-10-06       Impact factor: 8.542

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