Literature DB >> 11167698

Generalized dystrophic epidermolysis bullosa: identification of a novel, homozygous glycine substitution, G2031S, in exon 73 of COL7A1 in monozygous triplets.

E J Nordal1, S Mecklenbeck, I Hausser, J Skranes, L Bruckner-Tuderman, T Gedde-Dahl .   

Abstract

We report monozygous triplets affected with dystrophic epidermolysis bullosa (DEB). The female triplets were delivered by Caesarean section and skin fragility of each child, which was partly induced by trauma, was apparent from the third to fourth day of life. Clinically, the triplets were equally affected. Mutation analysis in this family revealed a novel recessively expressed glycine substitution, G2031S, in exon 73 of the collagen VII gene COL7A1. Most glycine substitutions in this gene region encoding for the triple helical domain of collagen VII are associated with milder, dominantly inherited phenotypes. By contrast, the novel point mutation of this study is clinically silent in the heterozygous state and leads to a severe DEB subtype when homozygous.

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Year:  2001        PMID: 11167698     DOI: 10.1046/j.1365-2133.2001.03966.x

Source DB:  PubMed          Journal:  Br J Dermatol        ISSN: 0007-0963            Impact factor:   9.302


  1 in total

1.  A novel deletion and two recurrent substitutions on type VII collagen gene in seven Iranian patients with epidermolysis bullosa.

Authors:  Armita Kakavand Hamidi; Mohammad Moghaddam; Nasim Hatamnejadian; Ahmad Ebrahimi
Journal:  Iran J Basic Med Sci       Date:  2016-08       Impact factor: 2.699

  1 in total

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