Literature DB >> 10953198

Phenotype-genotype correlation in eight patients with Finnish variant late infantile NCL (CLN5).

V Holmberg1, L Lauronen, T Autti, P Santavuori, M Savukoski, P Uvebrant, I Hofman, L Peltonen, I Järvelä.   

Abstract

The authors analyzed the clinical phenotype, including MRI, of eight patients with Finnish variant late infantile neuronal ceroid lipofuscinosis (vLINCLFin; CLN5; MIM256731). Although the four known mutations, including one novel mutation identified in this study, have very different consequences for the predicted polypeptide, none of them results in an atypical phenotype, as has been reported in other forms of NCL. Thus, it seems likely that each mutation severely disturbs the normal function of the CLN5 protein.

Entities:  

Mesh:

Substances:

Year:  2000        PMID: 10953198     DOI: 10.1212/wnl.55.4.579

Source DB:  PubMed          Journal:  Neurology        ISSN: 0028-3878            Impact factor:   9.910


  20 in total

Review 1.  The Finnish Disease Heritage III: the individual diseases.

Authors:  Reijo Norio
Journal:  Hum Genet       Date:  2003-03-08       Impact factor: 4.132

Review 2.  Progressive myoclonic epilepsies: review of clinical, molecular and therapeutic aspects.

Authors:  Luis Felipe Mendonça de Siqueira
Journal:  J Neurol       Date:  2010-07-01       Impact factor: 4.849

Review 3.  Correlations between genotype, ultrastructural morphology and clinical phenotype in the neuronal ceroid lipofuscinoses.

Authors:  Sara E Mole; Ruth E Williams; Hans H Goebel
Journal:  Neurogenetics       Date:  2005-09-28       Impact factor: 2.660

4.  An EEG Investigation of Sleep Homeostasis in Healthy and CLN5 Batten Disease Affected Sheep.

Authors:  Nicholas Perentos; Amadeu Q Martins; Robin J M Cumming; Nadia L Mitchell; David N Palmer; Stephen J Sawiak; A Jennifer Morton
Journal:  J Neurosci       Date:  2016-08-03       Impact factor: 6.167

Review 5.  Therapeutic approaches to the challenge of neuronal ceroid lipofuscinoses.

Authors:  R Kohan; I A Cismondi; A M Oller-Ramirez; N Guelbert; Tapia V Anzolini; G Alonso; S E Mole; Dodelson R de Kremer; Noher I de Halac
Journal:  Curr Pharm Biotechnol       Date:  2011-06       Impact factor: 2.837

Review 6.  Decreased T2 signal in the thalami may be a sign of lysosomal storage disease.

Authors:  Taina Autti; Raimo Joensuu; Laura Aberg
Journal:  Neuroradiology       Date:  2007-03-03       Impact factor: 2.804

7.  A new large animal model of CLN5 neuronal ceroid lipofuscinosis in Borderdale sheep is caused by a nucleotide substitution at a consensus splice site (c.571+1G>A) leading to excision of exon 3.

Authors:  Tony Frugier; Nadia L Mitchell; Imke Tammen; Peter J Houweling; Donald G Arthur; Graham W Kay; Otto P van Diggelen; Robert D Jolly; David N Palmer
Journal:  Neurobiol Dis       Date:  2007-09-29       Impact factor: 5.996

8.  Expanding the Neuroimaging Phenotype of Neuronal Ceroid Lipofuscinoses.

Authors:  A Biswas; P Krishnan; A Amirabadi; S Blaser; S Mercimek-Andrews; M Shroff
Journal:  AJNR Am J Neuroradiol       Date:  2020-08-27       Impact factor: 3.825

9.  Proteolytic processing of the neuronal ceroid lipofuscinosis related lysosomal protein CLN5.

Authors:  Bhagya De Silva; Jessie Adams; Stella Y Lee
Journal:  Exp Cell Res       Date:  2015-09-03       Impact factor: 3.905

Review 10.  Therapeutic landscape for Batten disease: current treatments and future prospects.

Authors:  Tyler B Johnson; Jacob T Cain; Katherine A White; Denia Ramirez-Montealegre; David A Pearce; Jill M Weimer
Journal:  Nat Rev Neurol       Date:  2019-03       Impact factor: 42.937

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.