| Literature DB >> 10925384 |
M Okubo1, A Horinishi, Y Suzuki, T Murase, K Hayasaka.
Abstract
Glycogen storage disease type III (GSD III) is an autosomal recessive disorder caused by deficiency of glycogen-debranching enzyme (AGL). We studied a 2-year-old GSD III patient whose parents were from different ethnic groups. Nucleotide sequence analysis of the patient showed two novel mutations: a single cytosine deletion at nucleotide 2399 (2399delC) in exon 16, and a G-to-A transition at the +5 position at the donor splice site of intron 33 (IVS33+5G>A). Analysis of the mRNA produced by IVS33+5G>A showed aberrant splicing: skipping of exon 33 and activation of a cryptic splice site in exon 34. Mutational analysis of the family revealed that the 2399delC was inherited from her father, who is of Japanese origin, and the IVS33+5G>A from her mother, who is of Chinese descent, establishing that the patient was a compound heterozygote. To our knowledge, this is the first report of a mutation identified in a GSD III patient from the Chinese population.Entities:
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Year: 2000 PMID: 10925384 DOI: 10.1002/1096-8628(20000731)93:3<211::aid-ajmg10>3.0.co;2-z
Source DB: PubMed Journal: Am J Med Genet ISSN: 0148-7299