Literature DB >> 10906521

Branchio-oculo-facial syndrome.

E Raveh1, B C Papsin, V Forte.   

Abstract

Branchio-oculo-facial (BOF) syndrome is a rare autosomal dominant disorder that has a distinct phenotype with characteristic craniofacial abnormalities. These consist of branchial anomalies, including supra-auricular sinuses, and aplastic cervical skin lesions, with possible ectopic dermal thymus, malformed auricles, stenotic external auditory canals, conductive hearing loss, ocular abnormalities (microphthalmia and lacrimal duct obstruction), and pseudocleft of the upper lip. Extracraniofacial malformations are uncommon. We describe two new cases of BOF and discuss the classical clinical presentation and differential diagnosis. Our two patients presented with facial nerve paralysis and were also were found to have inner ear dysplasias with associated sensorineural hearing loss which, to our knowledge, have not been described in the literature in association with this syndrome.

Entities:  

Mesh:

Year:  2000        PMID: 10906521     DOI: 10.1016/s0165-5876(00)00310-4

Source DB:  PubMed          Journal:  Int J Pediatr Otorhinolaryngol        ISSN: 0165-5876            Impact factor:   1.675


  6 in total

1.  FOXD1 Duplication Causes Branchial Defects and Interacts with the TFAP2A Gene Implicated in the Branchio-Oculo-Facial Syndrome in Causing Eye Effects in Zebrafish.

Authors:  I Balikova; K Devriendt; J-P Fryns; J R Vermeesch
Journal:  Mol Syndromol       Date:  2011-05-18

2.  A Case of Branchio-oculo-facial Syndrome.

Authors:  Min Young Park; You Chan Kim
Journal:  Ann Dermatol       Date:  2009-08-31       Impact factor: 1.444

3.  Branchio-oculo-facial syndrome.

Authors:  M L Kulkarni; Shilpa Deshmukh; Ananda Kumar; Preethi M Kulkarni
Journal:  Indian J Pediatr       Date:  2005-08       Impact factor: 1.967

Review 4.  Ocular manifestations of branchio-oculo-facial syndrome: report of a novel mutation and review of the literature.

Authors:  M S Al-Dosari; M Almazyad; L Al-Ebdi; J Y Mohamed; Saad Al-Dahmash; Hassan Al-Dhibi; Eman Al-Kahtani; Shahira Al-Turkmani; Hisham Alkuraya; B D Hall; F S Alkuraya
Journal:  Mol Vis       Date:  2010-05-08       Impact factor: 2.367

5.  Posterior Microphthalmia, Peripheral Pigmentary Retinal Changes, Yellow Lesions, and Cleft Lip: A Case Report and Literature Review.

Authors:  Nasser G Alsaedi; Khalid Alrubaie
Journal:  Case Rep Ophthalmol Med       Date:  2019-05-19

6.  Ocular coloboma combined with cleft lip and palate: a case report.

Authors:  Yung Ju Yoo; Sang Beom Han; Hee Kyung Yang; Jeong-Min Hwang
Journal:  BMC Ophthalmol       Date:  2020-10-19       Impact factor: 2.209

  6 in total

北京卡尤迪生物科技股份有限公司 © 2022-2023.