Literature DB >> 10878667

Segmental neurofibromatosis is caused by somatic mutation of the neurofibromatosis type 1 (NF1) gene.

S Tinschert1, I Naumann, E Stegmann, A Buske, D Kaufmann, G Thiel, D E Jenne.   

Abstract

Segmental neurofibromatosis (NF) is generally thought to result from a postzygotic NF1 (neurofibromatosis type 1) gene mutation. However, this has not yet been demonstrated at the molecular level. Using fluorescence in situ hybridisation (FISH) we identified an NF1 microdeletion in a patient with segmental NF in whom café-au-lait spots and freckles are limited to a single body region. The mutant allele was present in a mosaic pattern in cultured fibroblasts from a café-au-lait spot lesion, but was absent in fibroblasts from normal skin as well as in peripheral blood leukocytes. These findings prove the hypothesis that the molecular basis of segmental cutaneous NF is a mutation in the NF1 gene and that the regional distribution of manifestations reflects different cell clones, commensurate with the concept of somatic mosaicism.

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Year:  2000        PMID: 10878667     DOI: 10.1038/sj.ejhg.5200493

Source DB:  PubMed          Journal:  Eur J Hum Genet        ISSN: 1018-4813            Impact factor:   4.246


  32 in total

1.  Ophthalmological manifestations in segmental neurofibromatosis type 1.

Authors:  M Ruggieri; P Pavone; A Polizzi; M Di Pietro; A Scuderi; A Gabriele; A Spalice; P Iannetti
Journal:  Br J Ophthalmol       Date:  2004-11       Impact factor: 4.638

2.  Somatic mosaicism for a PDHA1 mutation in a female with pyruvate dehydrogenase deficiency.

Authors:  Cheryl K Ridout; Ruth M Brown; John H Walter; Garry K Brown
Journal:  Hum Genet       Date:  2008-08-17       Impact factor: 4.132

3.  Hereditary segmental neurofibromatosis: a report of three cases in a family.

Authors:  Rashmi Jindal; Nadia Shirazi; Kinnari Rawat
Journal:  BMJ Case Rep       Date:  2019-04-20

Review 4.  Mosaicism in Cutaneous Disorders.

Authors:  Young H Lim; Zoe Moscato; Keith A Choate
Journal:  Annu Rev Genet       Date:  2017-11-27       Impact factor: 16.830

5.  Molecular characterization and gene content of breakpoint boundaries in patients with neurofibromatosis type 1 with 17q11.2 microdeletions.

Authors:  D E Jenne; S Tinschert; H Reimann; W Lasinger; G Thiel; H Hameister; H Kehrer-Sawatzki
Journal:  Am J Hum Genet       Date:  2001-07-20       Impact factor: 11.025

6.  Monozygotic twins discordant for neurofibromatosis 1.

Authors:  Lee Kaplan; Rosemary Foster; Yiping Shen; Dilys M Parry; Mary L McMaster; Melanie Collins O'Leary; James F Gusella
Journal:  Am J Med Genet A       Date:  2010-03       Impact factor: 2.802

7.  [Rare form of a segmental neurofibromatosis with giant plexiform neurofibroma].

Authors:  Robin Reschke; Marketa Kadlecova; Sonja Grunewald; Mirjana Ziemer
Journal:  Hautarzt       Date:  2019-08       Impact factor: 0.751

Review 8.  Mosaic RASopathies.

Authors:  Christian Hafner; Leopold Groesser
Journal:  Cell Cycle       Date:  2012-12-19       Impact factor: 4.534

9.  A unique case of multiple non-ossifying fibromas with polyostotic monomelic distribution and aggressive clinical course.

Authors:  Alessandro Corsi; Cristina Remoli; Mara Riminucci; Ernesto Ippolito; John Dimitriou
Journal:  Skeletal Radiol       Date:  2016-11-08       Impact factor: 2.199

10.  Molecular dissection of isolated disease features in mosaic neurofibromatosis type 1.

Authors:  Ophélia Maertens; Sofie De Schepper; Jo Vandesompele; Hilde Brems; Ine Heyns; Sandra Janssens; Frank Speleman; Eric Legius; Ludwine Messiaen
Journal:  Am J Hum Genet       Date:  2007-06-20       Impact factor: 11.025

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