Literature DB >> 10730651

Tuberous sclerosis: differences between cerebral and cerebellar cortical tubers in a pediatric population.

L Martí-Bonmatí1, F Menor, R Dosdá.   

Abstract

BACKGROUND AND
PURPOSE: Histologic evidence of cortical tubers is pathognomonic of tuberous sclerosis (TS) disease. Cerebellar tubers, however, are uncommonly found. Our objective was to evaluate the prevalence and characteristics of cerebellar tubers in a large series of pediatric patients with TS studied with MR imaging. In particular, their relationship with volume loss and age will be analyzed.
METHODS: MR images of 34 children with TS and cortical tubers were reviewed. There were 17 female and 17 male patients. The mean age was 8.9+/-4.5 years (mean +/- SD), with a range from 2 to 14 years. The number and location (supratentorial, infratentorial) of tubers and volume loss of the underlying parenchyma were recorded. The relationship between tuber location, patient age, and number of tubers was studied using the Student's t test for independent samples. The relationship between tuber location and presence of volume loss was established using the Pearson chi2 test.
RESULTS: The mean number of cortical tubers was 14.3+/-8.5. Fifteen (44.1%) patients had cerebellar tubers associated with cerebral lesions. Patients with cerebellar and cerebral tubers had significantly more global cortical lesions than did patients with isolated cerebral tubers (17.9+/-8.9 versus 11.4+/-7.2 tubers, P = .026). Patients with cerebellar tubers were significantly older than those with isolated supratentorial tubers (11.3+/-3.4 versus 7.1+/-4.4 years, P = .005). In only four (11.8%) patients were tubers associated with focal parenchymal volume loss. The tubers in all of these cases were located in the cerebellum-indicating a significant relationship with volume loss (Pearson chi2 test, P = .017).
CONCLUSION: In this series, cerebellar tubers were frequent and were always present in association with cerebral cortical tubers. They were seen in older children with a larger total number of tubers. Cerebellar tubers may be associated with focal volume loss.

Entities:  

Mesh:

Year:  2000        PMID: 10730651      PMCID: PMC8175001     

Source DB:  PubMed          Journal:  AJNR Am J Neuroradiol        ISSN: 0195-6108            Impact factor:   3.825


  11 in total

1.  Imaging characteristics of tuberous sclerosis.

Authors:  D G Bell; B F King; R R Hattery; J W Charboneau; A D Hoffman; O W Houser
Journal:  AJR Am J Roentgenol       Date:  1991-05       Impact factor: 3.959

2.  Cerebral tuberous sclerosis: MR imaging.

Authors:  J R Nixon; O W Houser; M R Gomez; H Okazaki
Journal:  Radiology       Date:  1989-03       Impact factor: 11.105

3.  Tuberous sclerosis: characteristics at CT and MR imaging.

Authors:  N R Altman; R K Purser; M J Post
Journal:  Radiology       Date:  1988-05       Impact factor: 11.105

4.  The natural history of cardiac rhabdomyoma with and without tuberous sclerosis.

Authors:  G Bosi; J P Lintermans; P A Pellegrino; G Svaluto-Moreolo; A Vliers
Journal:  Acta Paediatr       Date:  1996-08       Impact factor: 2.299

5.  Cortical tuber count: a biomarker indicating neurologic severity of tuberous sclerosis complex.

Authors:  M Goodman; S H Lamm; A Engel; C W Shepherd; O W Houser; M R Gomez
Journal:  J Child Neurol       Date:  1997-02       Impact factor: 1.987

Review 6.  MR imaging of tuberous sclerosis: pathogenesis of this phakomatosis, use of gadopentetate dimeglumine, and literature review.

Authors:  B H Braffman; L T Bilaniuk; T P Naidich; N R Altman; M J Post; R M Quencer; R A Zimmerman; B A Brody
Journal:  Radiology       Date:  1992-04       Impact factor: 11.105

7.  Renal lesion growth in children with tuberous sclerosis complex.

Authors:  D H Ewalt; E Sheffield; S P Sparagana; M R Delgado; E S Roach
Journal:  J Urol       Date:  1998-07       Impact factor: 7.450

8.  Tuber and subependymal giant cell astrocytoma associated with tuberous sclerosis: an immunohistochemical, ultrastructural, and immunoelectron and microscopic study.

Authors:  T Hirose; B W Scheithauer; M B Lopes; H A Gerber; H J Altermatt; M J Hukee; S R VandenBerg; J C Charlesworth
Journal:  Acta Neuropathol       Date:  1995       Impact factor: 17.088

9.  Tuberous sclerosis: a clinicoradiological evaluation of 110 cases with particular reference to atypical presentation.

Authors:  D P Kingsley; B E Kendall; C R Fitz
Journal:  Neuroradiology       Date:  1986       Impact factor: 2.804

10.  Neuroimaging in tuberous sclerosis: a clinicoradiological evaluation in pediatric patients.

Authors:  F Menor; L Martí-Bonmatí; F Mulas; C Poyatos; H Cortina
Journal:  Pediatr Radiol       Date:  1992
View more
  12 in total

1.  MRI findings reveal three different types of tubers in patients with tuberous sclerosis complex.

Authors:  Anne Gallagher; Ellen P Grant; Neel Madan; Delma Y Jarrett; David A Lyczkowski; Elizabeth A Thiele
Journal:  J Neurol       Date:  2010-03-30       Impact factor: 4.849

2.  Unique findings of subependymal giant cell astrocytoma within cortical tubers in patients with tuberous sclerosis complex: a histopathological evaluation.

Authors:  Joel S Katz; Hyman Frankel; Tracy Ma; David Zagzag; Benjamin Liechty; Bruria Ben Zeev; Michal Tzadok; Orrin Devinsky; Howard L Weiner; Jonathan Roth
Journal:  Childs Nerv Syst       Date:  2017-01-10       Impact factor: 1.475

3.  Comparative analysis of MR sequences to detect structural brain lesions in tuberous sclerosis.

Authors:  Hugo Pereira Pinto Gama; Antônio José da Rocha; Flávio Túlio Braga; Carlos Jorge da Silva; Antonio Carlos Martins Maia; Rogério Gonçalves de Campos Meirelles; José Iram Mendonça do Rego; Henrique Manoel Lederman
Journal:  Pediatr Radiol       Date:  2005-11-11

Review 4.  Imaging genetics in neurodevelopmental psychopathology.

Authors:  Marieke Klein; Marjolein van Donkelaar; Ellen Verhoef; Barbara Franke
Journal:  Am J Med Genet B Neuropsychiatr Genet       Date:  2017-07       Impact factor: 3.568

5.  Transient mGlu5R inhibition enhances the survival of granule cell precursors in the neonatal cerebellum.

Authors:  C Kubera; A L Hernandez; V Heng; A Bordey
Journal:  Neuroscience       Date:  2012-06-04       Impact factor: 3.590

6.  Semi-automatic volumetry of cortical tubers in tuberous sclerosis complex.

Authors:  Yasuhiro Nakata; Noriko Sato; Ayako Hattori; Kimiteru Ito; Yukio Kimura; Kouhei Kamiya; Yoko Shigemoto; Eiji Nakagawa; Masayuki Sasaki; Kuni Ohtomo
Journal:  Jpn J Radiol       Date:  2013-02-02       Impact factor: 2.374

Review 7.  Cerebellar Development and Autism Spectrum Disorder in Tuberous Sclerosis Complex.

Authors:  Maria Sundberg; Mustafa Sahin
Journal:  J Child Neurol       Date:  2015-08-24       Impact factor: 1.987

8.  MRI characteristics of cerebellar tubers and their longitudinal changes in children with tuberous sclerosis complex.

Authors:  Razan Daghistani; James Rutka; Elysa Widjaja
Journal:  Childs Nerv Syst       Date:  2014-09-09       Impact factor: 1.475

9.  Cerebral diffusion tensor images in children with tuberous sclerosis: a preliminary report.

Authors:  Steven Shinn-Forng Peng; Wang-Tso Lee; Yao Hung Wang; Kou-Mou Huang
Journal:  Pediatr Radiol       Date:  2004-03-17

10.  MRI characterization and longitudinal study of focal cerebellar lesions in a young tuberous sclerosis cohort.

Authors:  J Vaughn; M Hagiwara; J Katz; J Roth; O Devinsky; H Weiner; S Milla
Journal:  AJNR Am J Neuroradiol       Date:  2012-09-06       Impact factor: 3.825

View more

北京卡尤迪生物科技股份有限公司 © 2022-2023.