Literature DB >> 10571348

Posterior scleral choristoma in the organoid nevus syndrome (linear nevus sebaceus of Jadassohn).

E I Traboulsi1, A Zin, S J Massicotte, G Kosmorsky, P Kotagal, F D Ellis.   

Abstract

PURPOSE: To highlight the association of posterior osseous and/or cartilaginous ocular choristomas with epibulbar choristomas and the nevus sebaceus of Jadassohn.
DESIGN: Small case series. PARTICIPANTS: Four patients with the organoid nevus syndrome.
METHODS: Clinical and histopathologic studies in four patients with epibulbar lesions and nevus sebaceus of Jadassohn. MAIN OUTCOME MEASURES: Ophthalmoscopic findings of peripapillary lesions. Computed tomographic and ultrasonographic characteristic of posterior scleral lesions. Ocular histopathologic findings in one globe from one of the study subjects.
RESULTS: Three patients had the triad of posterior osseous/cartilaginous ocular choristomas, anterior epibulbar choristomas, and nevus sebaceus of Jadassohn and one patient had anterior epibulbar choristomas and posterior osseous/cartilaginous ocular choristomas. Ultrasonography and computed tomography were valuable in detecting scleral ossification or epibulbar cartilage or both. The ophthalmoscopic findings were similar to those of a choroidal osteoma.
CONCLUSIONS: The presence of posterior osseous/cartilaginous ocular choristomas in a patient with epilepsy or epibulbar lesions or both suggests the diagnosis of nevus sebaceus of Jadassohn. Osseous/cartilaginous ocular choristomas should be suspected in patients with nevus sebaceus of Jadassohn and peripapillary hypopigmented fundus lesions.

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Year:  1999        PMID: 10571348     DOI: 10.1016/S0161-6420(99)90494-3

Source DB:  PubMed          Journal:  Ophthalmology        ISSN: 0161-6420            Impact factor:   12.079


  4 in total

Review 1.  A case of epibulbar osseous choristoma with review of literature.

Authors:  Ozlem Balci; Abdulkadir Oduncu
Journal:  Int Ophthalmol       Date:  2014-05-06       Impact factor: 2.031

2.  Epidermal nevus syndrome associated with anterior scleral staphyloma and ectopic bone and cartilaginous intraocular tissue.

Authors:  Yasuhiro Miyagawa; Mitsuru Nakazawa; Takashi Kudoh
Journal:  Jpn J Ophthalmol       Date:  2010-02-12       Impact factor: 2.447

3.  The retinal pigment epithelium of the eye regulates the development of scleral cartilage.

Authors:  H Thompson; J S Griffiths; G Jeffery; I M McGonnell
Journal:  Dev Biol       Date:  2010-08-11       Impact factor: 3.582

4.  Epibulbar complex and osseous choristoma: Clinicopathological study with interesting associations.

Authors:  Mohammed M Aldossary; Hind M Alkatan; Azza My Maktabi
Journal:  Ann Med Surg (Lond)       Date:  2018-10-31
  4 in total

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