Literature DB >> 10434308

Androgen receptor mutation in Kennedy's disease.

K H Fischbeck1, A Lieberman, C K Bailey, A Abel, D E Merry.   

Abstract

Kennedy's disease is an X-linked form of motor neuron disease caused by an expanded polyglutamine repeat in the androgen receptor. While the expansion mutation causes some loss of transcriptional activity by the androgen receptor, the predominant effect of expansion is probably a toxic gain of function, similar to the mechanism of other polyglutamine expansion diseases. Features of the neurodegenerative phenotype of Kennedy's disease have now been reproduced in transgenic animals and neuronal cell culture. Nuclear inclusions of mutant androgen receptor protein are found in these model systems and in autopsy samples from patients with Kennedy's disease.

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Year:  1999        PMID: 10434308      PMCID: PMC1692603          DOI: 10.1098/rstb.1999.0461

Source DB:  PubMed          Journal:  Philos Trans R Soc Lond B Biol Sci        ISSN: 0962-8436            Impact factor:   6.237


  23 in total

1.  Androgen receptor gene mutations in X-linked spinal and bulbar muscular atrophy.

Authors:  A R La Spada; E M Wilson; D B Lubahn; A E Harding; K H Fischbeck
Journal:  Nature       Date:  1991-07-04       Impact factor: 49.962

2.  Meiotic stability and genotype-phenotype correlation of the trinucleotide repeat in X-linked spinal and bulbar muscular atrophy.

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Journal:  Nat Genet       Date:  1992-12       Impact factor: 38.330

3.  Kennedy's disease: caspase cleavage of the androgen receptor is a crucial event in cytotoxicity.

Authors:  L M Ellerby; A S Hackam; S S Propp; H M Ellerby; S Rabizadeh; N R Cashman; M A Trifiro; L Pinsky; C L Wellington; G S Salvesen; M R Hayden; D E Bredesen
Journal:  J Neurochem       Date:  1999-01       Impact factor: 5.372

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Authors:  M Sar; W E Stumpf
Journal:  Science       Date:  1977-07-01       Impact factor: 47.728

5.  Progressive proximal spinal and bulbar muscular atrophy of late onset. A sex-linked recessive trait.

Authors:  W R Kennedy; M Alter; J H Sung
Journal:  Neurology       Date:  1968-07       Impact factor: 9.910

6.  X-linked recessive bulbospinal neuronopathy. A clinicopathological study.

Authors:  G Sobue; Y Hashizume; E Mukai; M Hirayama; T Mitsuma; A Takahashi
Journal:  Brain       Date:  1989-02       Impact factor: 13.501

7.  Reduced androgen receptor gene expression with first exon CAG repeat expansion.

Authors:  C S Choong; J A Kemppainen; Z X Zhou; E M Wilson
Journal:  Mol Endocrinol       Date:  1996-12

8.  Administration of testosterone attenuates neuronal loss following axotomy in the brain-stem motor nuclei of female rats.

Authors:  W H Yu
Journal:  J Neurosci       Date:  1989-11       Impact factor: 6.167

9.  Stability of an expanded trinucleotide repeat in the androgen receptor gene in transgenic mice.

Authors:  P M Bingham; M O Scott; S Wang; M J McPhaul; E M Wilson; J Y Garbern; D E Merry; K H Fischbeck
Journal:  Nat Genet       Date:  1995-02       Impact factor: 38.330

10.  Reduced transcriptional regulatory competence of the androgen receptor in X-linked spinal and bulbar muscular atrophy.

Authors:  A N Mhatre; M A Trifiro; M Kaufman; P Kazemi-Esfarjani; D Figlewicz; G Rouleau; L Pinsky
Journal:  Nat Genet       Date:  1993-10       Impact factor: 38.330

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  18 in total

Review 1.  Modifiers and mechanisms of multi-system polyglutamine neurodegenerative disorders: lessons from fly models.

Authors:  Moushami Mallik; Subhash C Lakhotia
Journal:  J Genet       Date:  2010-12       Impact factor: 1.166

2.  Androgen-dependent pathology demonstrates myopathic contribution to the Kennedy disease phenotype in a mouse knock-in model.

Authors:  Zhigang Yu; Nahid Dadgar; Megan Albertelli; Kirsten Gruis; Cynthia Jordan; Diane M Robins; Andrew P Lieberman
Journal:  J Clin Invest       Date:  2006-09-14       Impact factor: 14.808

3.  Abnormalities of germ cell maturation and sertoli cell cytoskeleton in androgen receptor 113 CAG knock-in mice reveal toxic effects of the mutant protein.

Authors:  Zhigang Yu; Nahid Dadgar; Megan Albertelli; Arno Scheller; Roger L Albin; Diane M Robins; Andrew P Lieberman
Journal:  Am J Pathol       Date:  2006-01       Impact factor: 4.307

4.  Pharmacological induction of heat-shock proteins alleviates polyglutamine-mediated motor neuron disease.

Authors:  Masahisa Katsuno; Chen Sang; Hiroaki Adachi; Makoto Minamiyama; Masahiro Waza; Fumiaki Tanaka; Manabu Doyu; Gen Sobue
Journal:  Proc Natl Acad Sci U S A       Date:  2005-10-31       Impact factor: 11.205

Review 5.  New insight into neurodegeneration: the role of proteomics.

Authors:  Ramavati Pal; Guido Alves; Jan Petter Larsen; Simon Geir Møller
Journal:  Mol Neurobiol       Date:  2013-12-10       Impact factor: 5.590

Review 6.  Pathogenic mechanisms and therapeutic strategies in spinobulbar muscular atrophy.

Authors:  Jason P Chua; Andrew P Lieberman
Journal:  CNS Neurol Disord Drug Targets       Date:  2013-12       Impact factor: 4.388

7.  The androgen receptor's CAG/glutamine tract in mouse models of neurological disease and cancer.

Authors:  Andrew P Lieberman; Diane M Robins
Journal:  J Alzheimers Dis       Date:  2008-06       Impact factor: 4.472

8.  Abnormal eye movements in Kennedy disease.

Authors:  Matthew J Thurtell; Erik P Pioro; R John Leigh
Journal:  Neurology       Date:  2009-04-28       Impact factor: 9.910

9.  The role of androgen receptor activity mediated by the CAG repeat polymorphism in the pathogenesis of PCOS.

Authors:  N Baculescu
Journal:  J Med Life       Date:  2013-03-25

10.  Amplification of GC-rich Putative Mouse PeP Promoter using Betaine and DMSO in Ammonium Sulfate Polymerase Chain Reaction Buffer.

Authors:  Tahere Seifi; Kamran Ghaedi; Ahmad Salamian; Sommayeh Tanhaei; Forouzan Safari; Zohreh Hojati; Manuchehr Tavassoli; Hossein Baharvand; Mohammad-Hossein Nasr Esfahani
Journal:  Avicenna J Med Biotechnol       Date:  2012-10
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