Literature DB >> 10083738

A novel nonsense mutation of the PEX7 gene in a patient with rhizomelic chondrodysplasia punctata.

N Shimozawa1, Y Suzuki, Z Zhang, K Miura, A Matsumoto, M Nagaya, S Castillo-Taucher, N Kondo.   

Abstract

Mutations in the PEX7 gene encoding a peroxisome targeting signal 2 (PTS2) were identified in two patients with rhizomelic chondrodysplasia punctata (RCDP). A 7-year-old girl, the first Japanese individual to be diagnosed biochemically as a case of RCDP, had a novel nonsense mutation, R232ter, in the PEX7 gene, which had been inherited from her consanguineous parents. Another patient, a Chilean boy with RCDP, had compound heterozygous mutations of PEX7, L292ter and A218V, both of which have been documented. R232ter, which deletes all of the last two WP40 repeats in the PEX7 gene, is sufficient to inactivate functions of the PEX7 gene.

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Year:  1999        PMID: 10083738     DOI: 10.1007/s100380050123

Source DB:  PubMed          Journal:  J Hum Genet        ISSN: 1434-5161            Impact factor:   3.172


  4 in total

1.  Mutational spectrum in the PEX7 gene and functional analysis of mutant alleles in 78 patients with rhizomelic chondrodysplasia punctata type 1.

Authors:  Alison M Motley; Pedro Brites; Lisya Gerez; Eveline Hogenhout; Janet Haasjes; Rob Benne; Henk F Tabak; Ronald J A Wanders; Hans R Waterham
Journal:  Am J Hum Genet       Date:  2002-01-07       Impact factor: 11.025

2.  Defective lipid remodeling of GPI anchors in peroxisomal disorders, Zellweger syndrome, and rhizomelic chondrodysplasia punctata.

Authors:  Noriyuki Kanzawa; Nobuyuki Shimozawa; Ronald J A Wanders; Kazutaka Ikeda; Yoshiko Murakami; Hans R Waterham; Satoru Mukai; Morihisa Fujita; Yusuke Maeda; Ryo Taguchi; Yukio Fujiki; Taroh Kinoshita
Journal:  J Lipid Res       Date:  2012-01-17       Impact factor: 5.922

3.  Posttranslational regulation of fatty acyl-CoA reductase 1, Far1, controls ether glycerophospholipid synthesis.

Authors:  Masanori Honsho; Shunsuke Asaoku; Yukio Fujiki
Journal:  J Biol Chem       Date:  2010-01-13       Impact factor: 5.157

4.  Whole Exome Sequencing Reveals Compound Heterozygosity for Ethnically Distinct PEX7 Mutations Responsible for Rhizomelic Chondrodysplasia Punctata, Type 1.

Authors:  Jessie C Jacobsen; Emma Glamuzina; Juliet Taylor; Brendan Swan; Shona Handisides; Callum Wilson; Michael Fietz; Tessa van Dijk; Bart Appelhof; Rosamund Hill; Rosemary Marks; Donald R Love; Stephen P Robertson; Russell G Snell; Klaus Lehnert
Journal:  Case Rep Genet       Date:  2015-10-26
  4 in total

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